Abstract
The study describes the mutations causing adrenoleukodystrophy in seven Italian families. Four missense mutations leading to amino acid substitutions, two frameshift mutations leading to a premature termination signal, and a splicing mutation were identified. Mutations 2014C>T (P543L), 2053A>G (Q556A), 673-674insCC, and 1874+1G>A are described for the first time in this report. Mutations 1638C>T (R418W), 1588G>A(R401Q), and 1801-1802delAG are already known to be link to ALD.
Copyright 2000 Wiley-Liss, Inc.
MeSH terms
-
ATP Binding Cassette Transporter, Subfamily D, Member 1
-
ATP-Binding Cassette Transporters / genetics*
-
Adrenoleukodystrophy / enzymology
-
Adrenoleukodystrophy / genetics*
-
Adult
-
Amino Acid Substitution / genetics
-
Child
-
Coenzyme A Ligases / genetics
-
Exons / genetics
-
Female
-
Frameshift Mutation / genetics
-
Humans
-
Male
-
Membrane Proteins / genetics*
-
Mutation / genetics*
-
Mutation, Missense / genetics
-
Pedigree
-
Repressor Proteins*
-
Saccharomyces cerevisiae Proteins*
-
Sequence Analysis, DNA
Substances
-
ABCD1 protein, human
-
ATP Binding Cassette Transporter, Subfamily D, Member 1
-
ATP-Binding Cassette Transporters
-
Membrane Proteins
-
Repressor Proteins
-
Saccharomyces cerevisiae Proteins
-
Coenzyme A Ligases
-
FAA2 protein, S cerevisiae
-
long-chain-fatty-acid-CoA ligase