In vitro fertilization and the cloacal-bladder exstrophy-epispadias complex: is there an association?

J Urol. 2003 Apr;169(4):1512-5. doi: 10.1097/01.ju.0000054984.76384.66.

Abstract

Purpose: The cloacal-bladder exstrophy-epispadias complex represents a collection of congenital malformations caused by failed mesenchymal development during the first trimester. We sought to determine whether the exstrophy-epispadias complex is overrepresented among children conceived by in vitro fertilization (IVF).

Materials and methods: The clinic charts of all patients born between 1998 and 2001 who presented to our institution with the exstrophy-epispadias complex were reviewed. Four patients conceived by IVF and born with exstrophy-epispadias were identified and telephone interviews were conducted with the parents. Statistical analysis using clinical data and available United States population data was performed.

Results: Of 78 clinic patients with exstrophy-epispadias born during a 4-year period 4 were conceived using IVF. An estimated 12% to 14% of children born in the United States with the exstrophy-epispadias complex are evaluated annually at our institution. During the years 1997 to 2000, 112,137 children in the United States were conceived using IVF. According to published incidence data, approximately 5 children with exstrophy-epispadias would be expected among this entire population. Expected numbers of children in the United States conceived by IVF and born with exstrophy-epispadias during a 4-year period were calculated based on the observed number in our clinic population. A resulting 7.3-fold relative increase in incidence was determined (p = 0.0021).

Conclusions: The exstrophy-epispadias complex appears to occur more frequently in children conceived by in vitro fertilization.

MeSH terms

  • Bladder Exstrophy / epidemiology
  • Bladder Exstrophy / etiology*
  • Child, Preschool
  • Cross-Sectional Studies
  • Epispadias / epidemiology
  • Epispadias / etiology*
  • Female
  • Fertilization in Vitro* / statistics & numerical data
  • Follow-Up Studies
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Pregnancy
  • Retrospective Studies
  • Risk Assessment