[Phenotype of patients showing hearing impairment based on the 35delG mutation in the connexin 26 gene]

HNO. 2003 May;51(5):400-4. doi: 10.1007/s00106-002-0737-2. Epub 2003 Mar 27.
[Article in German]

Abstract

Background: Hereditary hearing impairment constitutes a heterogeneous class of disorders showing different patterns of inheritance and involving multiple genes. Mutations in the GJB2 gene, especially the 35delG mutation, have been established as a major cause of inherited and sporadic nonsyndromic hearing impairment in different populations.

Methods: We analyzed 14 northeast Hungarian families and 69 sporadic cases with nonsyndromic hearing impairment for the 35delG mutation. Sixty-five patients showing a homozygous 35delG mutation were examined regarding their audiologic phenotype.

Results: In general, these patients (70%) showed a prelingual, sensorineural, bilateral, symmetric hearing impairment without progression. The audiograms demonstrated sloping as well as flat patterns.

Conclusions: The severity of hearing impairment varied in 30% of all analyzed patients, making genetic counseling difficult.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acoustic Impedance Tests
  • Adolescent
  • Adult
  • Aged
  • Audiometry, Pure-Tone
  • Child
  • Child, Preschool
  • Chromosome Deletion*
  • Codon, Terminator / genetics
  • Connexin 26
  • Connexins / genetics*
  • DNA Mutational Analysis
  • Deafness / diagnosis
  • Deafness / genetics*
  • Disease Progression
  • Female
  • Frameshift Mutation / genetics
  • Genetic Carrier Screening
  • Guanine / metabolism
  • Homozygote*
  • Humans
  • Male
  • Middle Aged
  • Phenotype*

Substances

  • Codon, Terminator
  • Connexins
  • GJB2 protein, human
  • Connexin 26
  • Guanine