Toriello-Carey syndrome associated with respiratory failure and non-mechanical ileus

Am J Med Genet A. 2003 Aug 1;120A(4):537-41. doi: 10.1002/ajmg.a.20094.

Abstract

Toriello-Carey syndrome comprises agenesis of the corpus callosum, telecanthus, small palpebral fissures, Pierre Robin sequence, abnormal ears, and cardiac defects. We report a boy who has some additional findings, including a severe respiratory failure and intestinal dysmotility. The boy died of these two disorders at age 13 months. Histological examination revealed pulmonary immaturity and a defect of smooth muscle cells in the longitudinal muscle coat of the intestinal musculature, both of which might explain some aspects of the pathophysiology of the patient.

Publication types

  • Case Reports
  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Abnormalities, Multiple / pathology*
  • Agenesis of Corpus Callosum*
  • Fatal Outcome
  • Female
  • Humans
  • Ileus / pathology*
  • Infant
  • Intestine, Small / pathology*
  • Intestine, Small / ultrastructure
  • Lung / pathology
  • Lung / ultrastructure
  • Magnetic Resonance Imaging
  • Male
  • Respiratory Insufficiency / pathology*
  • Syndrome