[Mitochondrial A1555G mutation. Molecular genetic diagnosis in sporadic cases of non-syndromic hearing impairment]

HNO. 2004 Nov;52(11):968-72. doi: 10.1007/s00106-003-0994-8.
[Article in German]

Abstract

Background: The A1555G mutation in mitochondrial DNA is the cause of hearing impairment in about 50% of all carriers. The severity and onset of this impairment is predominantly affected by the use of aminoglycosides.

Patients and methods: A total of 391 patients displaying sporadic, non-syndromic, mild to severe hearing impairment were analyzed for the A1555G mutation using molecular genetic methods.

Results: We analysed additional family members of the two patients (0.5% of the total) who had the mutation. All maternal relatives carried the mutation, but only three individuals from the two families displayed a variable sensorineural hearing loss.

Conclusion: The A1555G mutation is infrequently involved as a genetic cause of sporadic, non-syndromic hearing impairment. Nevertheless, based on the variable clinical outcome of hearing impairment and the possibility of preventive steps, a genetic test in this patient subgroup is indicated.

Publication types

  • Case Reports
  • Clinical Trial
  • English Abstract

MeSH terms

  • DNA Mutational Analysis / methods
  • DNA, Mitochondrial / genetics
  • Genetic Predisposition to Disease / epidemiology*
  • Genetic Testing / methods*
  • Germany / epidemiology
  • Hearing Loss / epidemiology*
  • Hearing Loss / genetics*
  • Humans
  • Male
  • Mutation
  • Pedigree
  • Polymorphism, Genetic*
  • RNA, Ribosomal / genetics*
  • Risk Assessment / methods*
  • Risk Factors

Substances

  • DNA, Mitochondrial
  • RNA, Ribosomal
  • RNA, ribosomal, 12S