Camptodactyly, arthropathy, coxa vara, pericarditis (CACP)syndrome: a case report

J Korean Med Sci. 2004 Dec;19(6):907-10. doi: 10.3346/jkms.2004.19.6.907.

Abstract

The camptodactyly-arthropathy-coxa vara-pericarditis syndrome (CACP) is characterized by congenital or early-onset camptodactyly, childhood-onset noninflammatory arthropathy associated with synovial hyperplasia. Some patients have progressive coxa vara deformity and/or noninflammatory pericardial effusion. CACP is inherited as an autosomal recessive mode and the disease gene is assigned to a 1.9-cM interval on human chromosome 1q25-31. We describe a 10-yr-old boy who has typical features of CACP without familial association.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Fingers / abnormalities*
  • Hip Joint / abnormalities*
  • Humans
  • Joint Diseases / congenital*
  • Joint Diseases / diagnosis*
  • Male
  • Pericarditis / congenital*
  • Pericarditis / diagnosis*
  • Syndrome
  • Toes / abnormalities*