Diagnosis of Hirschsprung's disease: a prospective, comparative accuracy study of common tests

J Pediatr. 2005 Jun;146(6):787-92. doi: 10.1016/j.jpeds.2005.01.044.

Abstract

Objective: To compare the diagnostic accuracy of contrast enema (CE), anorectal manometry (ARM), and rectal suction biopsy (RSB) for the detection of Hirschsprung's disease (HD).

Study design: Following a prospective protocol, infants suspected of HD underwent all 3 index tests. Children with positive results on 2 or more index tests or who continued to have severe bowel problems underwent a full thickness biopsy as reference standard. Clinical follow-up was the reference standard in all other children.

Results: Between 2000 and 2003, 111 consecutive patients (67 boys; median age, 5.3 months) in whom HD was suspected were enrolled. HD was found in 28 patients. RSB had the highest sensitivity (93%) and specificity (100%) rates, but values were not significantly different from CE (sensitivity, 76%; specificity, 97%) or from ARM (sensitivity, 83%; specificity, 93%). Inconclusive test results occurred in 8 infants with CE, in 15 infants with ARM because of agitation, and in 2 infants with RSB.

Conclusion: RSB is the most accurate test for diagnosing HD, and it has the lowest rate of inconclusive test results.

Publication types

  • Comparative Study

MeSH terms

  • Anal Canal / pathology*
  • Biopsy / methods
  • Child
  • Child, Preschool
  • Contrast Media
  • Diatrizoate Meglumine
  • Enema*
  • Female
  • Follow-Up Studies
  • Hirschsprung Disease / diagnosis*
  • Hirschsprung Disease / surgery
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Manometry
  • Predictive Value of Tests
  • Prospective Studies
  • Rectum / pathology*
  • Sensitivity and Specificity
  • Suction

Substances

  • Contrast Media
  • Diatrizoate Meglumine