Nephrotic syndrome and renal failure after allogeneic stem cell transplantation: novel molecular diagnostic tools for a challenging differential diagnosis

Am J Kidney Dis. 2005 Sep;46(3):550-6. doi: 10.1053/j.ajkd.2005.05.026.

Abstract

Background: Sudden onset of nephrotic syndrome after allogeneic stem cell transplantation is rare and has been associated mostly with membranous glomerulonephritis related to chronic graft-versus-host disease (cGVHD). We report a case of nephrotic syndrome and rapidly progressive renal failure occurring in a young woman 3 years after allogeneic stem cell transplantation from her HLA-identical brother. In the renal biopsy, a diffuse mononuclear cell infiltrate was observed. Furthermore, histological analysis, immunofluorescence, and electron microscopy of the kidney specimen defined the diagnosis as minimal change disease, a T-cell-mediated glomerulopathy associated with lymphoproliferative disorders, but that has never been described as an isolated manifestation of cGVHD.

Methods: The differential diagnosis was performed by using immunohistochemistry and laser capture microdissection combined with Taq-Man quantitative polymerase chain reaction.

Results: Infiltrating mononuclear cells in renal tissue consisted of T cells expressing DNA levels of a Y chromosome-specific gene quantitatively similar to those observed in a male subject, showing that these cells derived from the transplant donor and definitely excluding leukemia relapse. However, the large number of infiltrating T cells allowed the possibility that in this patient, minimal change disease could be related to an atypical form of GVHD.

Conclusion: This is the first study to use molecular techniques to show the differential diagnosis of nephrotic syndrome after allogeneic stem cell transplantation. This novel method approach might represent a key tool to characterize kidney infiltrate after allogeneic stem cell transplantation.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acute Kidney Injury / diagnosis*
  • Acute Kidney Injury / etiology
  • Adult
  • CD8-Positive T-Lymphocytes / chemistry
  • CD8-Positive T-Lymphocytes / immunology
  • CD8-Positive T-Lymphocytes / transplantation*
  • Chromosomes, Human, Y / genetics
  • DNA / analysis
  • Diagnosis, Differential
  • Disease Progression
  • Female
  • Genetic Markers
  • Graft vs Host Disease / diagnosis*
  • Graft vs Host Disease / etiology
  • Humans
  • Kidney / pathology*
  • Leukemic Infiltration / diagnosis
  • Living Donors
  • Male
  • Nephrosis, Lipoid / diagnosis*
  • Nephrosis, Lipoid / etiology
  • Nephrotic Syndrome / diagnosis*
  • Nephrotic Syndrome / etiology
  • Peripheral Blood Stem Cell Transplantation / adverse effects*
  • Polymerase Chain Reaction
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / surgery
  • Transplantation, Homologous / adverse effects*
  • Transplantation, Homologous / immunology

Substances

  • Genetic Markers
  • DNA