Outcome for children <4 years of age with malignant central nervous system tumors treated with high-dose chemotherapy and autologous stem cell rescue

Pediatr Blood Cancer. 2007 Mar;48(3):278-84. doi: 10.1002/pbc.20781.

Abstract

Background: Children <4 years of age (yo) with malignant central nervous system (CNS) tumors have a dismal prognosis. In an attempt to delay or obviate radiation therapy (XRT) and improve outcome, our institution has treated children <4 yo with newly diagnosed malignant CNS tumors with high-dose chemotherapy (HDC) and autologous stem cell rescue (ASCR) followed by selective XRT.

Procedure: Fifteen children (age 4-38 months) with malignant CNS tumors have completed treatment with HDC/ASCR. All patients received three cycles of induction chemotherapy (cisplatin 3.5 mg/kg- day 0, cyclophosphamide 60 mg/kg- day 1 and 2, etoposide 2.5 mg/kg- day 0-2, vincristine 0.05 mg/kg, day 0, 7, 14) followed by three cycles of HDC (carboplatin 17 mg/kg and thiotepa 6 mg/kg, day 0 and 1) with ASCR. Histology included five medulloblastomas, four primitive neuroectodermal tumors (PNET), five malignant gliomas, and one ependymoma. Outcome and treatment toxicities were evaluated by retrospective chart review.

Results: Median follow-up time of the 15 patients is 22 months (range 8-82 months). The 1- and 2-year progression-free survival (PFS) is 86.1% and 52.2% and overall survival (OS) 91.6% and 72.1%, respectively. Ten patients are alive and disease free 3-77 months (median 18 months) after having completed HDC/ASCR, thereoff five received XRT. Toxicity was primarily myelosuppression. There was no treatment mortality.

Conclusions: We are encouraged by the outcome of 15 children <4 yo with malignant CNS tumors treated with tandem cycles of HDC and ASCR at our institution. The treatment regimen is relatively well tolerated.

MeSH terms

  • Antineoplastic Combined Chemotherapy Protocols / adverse effects
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use*
  • Brain Neoplasms / complications
  • Brain Neoplasms / drug therapy
  • Brain Neoplasms / mortality
  • Brain Neoplasms / radiotherapy
  • Brain Neoplasms / surgery
  • Brain Neoplasms / therapy*
  • Carboplatin / administration & dosage
  • Child, Preschool
  • Cisplatin / administration & dosage
  • Cognition Disorders / etiology
  • Cranial Irradiation / adverse effects
  • Cyclophosphamide / administration & dosage
  • Developmental Disabilities / etiology
  • Disease-Free Survival
  • Ependymoma / drug therapy
  • Ependymoma / mortality
  • Ependymoma / surgery
  • Etoposide / administration & dosage
  • Follow-Up Studies
  • Ganglioglioma / drug therapy
  • Ganglioglioma / metabolism
  • Ganglioglioma / radiotherapy
  • Ganglioglioma / surgery
  • Glioma / drug therapy
  • Glioma / mortality
  • Glioma / radiotherapy
  • Glioma / surgery
  • Humans
  • Infant
  • Medulloblastoma / drug therapy
  • Medulloblastoma / mortality
  • Medulloblastoma / radiotherapy
  • Medulloblastoma / surgery
  • Mitotic Index
  • Neuroectodermal Tumors, Primitive / drug therapy
  • Neuroectodermal Tumors, Primitive / mortality
  • Neuroectodermal Tumors, Primitive / radiotherapy
  • Neuroectodermal Tumors, Primitive / surgery
  • Oligodendroglioma / drug therapy
  • Oligodendroglioma / mortality
  • Oligodendroglioma / surgery
  • Oligodendroglioma / therapy*
  • Peripheral Blood Stem Cell Transplantation* / adverse effects
  • Quadriplegia / etiology
  • Retrospective Studies
  • Sensation Disorders / etiology
  • Spinal Cord Neoplasms / drug therapy
  • Spinal Cord Neoplasms / surgery
  • Thiotepa / administration & dosage
  • Transplantation, Autologous
  • Treatment Outcome
  • Vincristine / administration & dosage

Substances

  • Vincristine
  • Etoposide
  • Cyclophosphamide
  • Thiotepa
  • Carboplatin
  • Cisplatin