Diagnosis of paroxysmal nocturnal hemoglobinuria by fluorescent clostridium septicum alpha toxin

J Mol Microbiol Biotechnol. 2006;11(1-2):20-7. doi: 10.1159/000092816.

Abstract

Paroxysmal nocturnal hemoglobinuria (PNH), a hematopoietic stem cell disorder, is caused by the loss of glycosylphosphatidylinositol (GPI)-anchored proteins on the cell membrane. PNH can be simply diagnosed by flow cytometry using monoclonal antibodies against GPI-anchored proteins or fluorescent-tagged aerolysin, a bacterial toxin that binds GPI anchored proteins. Clostridium septicum alpha toxin is homologous to aerolysin and specifically binds GPI-anchored proteins. Previously, we found that an alpha toxin m45 mutant with two amino acid changes, S189C/S238C, lost cytotoxicity but still possessed binding activity for GPI-anchored proteins. To use this mutant toxin as a diagnostic probe in flow cytometry, we constructed the EGFP-AT(m45) expression vector, comprising a S189C/S238C alpha toxin mutant with EGFP and His tags at the N and C termini, respectively. The recombinant EGFP-AT(m45) was easily purified using single-step affinity chromatography against His tag from Escherichia coli. EGFP-AT(m45) bound to CHO and HeLa cells in a similar manner to monoclonal antibodies against GPI-anchored proteins or aerolysin. In whole blood from a PNH patient, GPI-deficient granulocytes could be differentiated by EGFP-AT(m45) using the same procedure as that employed with commercially available monoclonal antibodies. Therefore, nontoxic EGFP-conjugated C. septicum alpha toxin could be used clinically for PNH diagnosis.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Antibodies, Monoclonal
  • Bacterial Toxins / genetics*
  • CD55 Antigens / immunology
  • CD59 Antigens / immunology
  • CHO Cells
  • Cell Survival
  • Cricetinae
  • Cricetulus
  • Flow Cytometry
  • Granulocytes / metabolism
  • Granulocytes / pathology
  • Green Fluorescent Proteins / genetics
  • HeLa Cells
  • Hemoglobinuria, Paroxysmal / blood
  • Hemoglobinuria, Paroxysmal / diagnosis*
  • Humans
  • Mutation
  • Recombinant Fusion Proteins* / genetics
  • Recombinant Fusion Proteins* / metabolism

Substances

  • Antibodies, Monoclonal
  • Bacterial Toxins
  • CD55 Antigens
  • CD59 Antigens
  • Recombinant Fusion Proteins
  • enhanced green fluorescent protein
  • hemolytic toxin, Clostridium septicum
  • Green Fluorescent Proteins