Autoantibody response to BPI predict disease severity and outcome in cystic fibrosis

J Cyst Fibros. 2007 May;6(3):228-33. doi: 10.1016/j.jcf.2006.10.005. Epub 2006 Dec 12.

Abstract

Background: Autoantibodies against bactericidal permeability increasing protein (BPI-ANCA) are frequently present in cystic fibrosis patients and have been reported to be associated to colonization with Pseudomonas (P) aeruginosa and lung damage. In the present study, we investigated BPI-ANCA as a prognostic marker and its relation to P. aeruginosa colonization and lung function.

Methods: BPI-ANCA, measured by ELISA, was examined relative to lung function and microbiological findings. The prognostic value of BPI-ANCA was assessed in 46 adult patients followed for 1.2-8.9 years. The cross-sectional investigation was performed in 366 patients (age 0.5-55).

Results: The presence of BPI-ANCA predicted poor prognosis. An adverse outcome occurred in 15/28 BPI-ANCA positive patients and in 2/18 BPI-ANCA negative patients (p=0.01). This result remained valid when the patients were stratified according to lung function (p=0.03). Findings of BPI-ANCA were correlated to P. aeruginosa colonization and lung damage. Development of BPI-ANCA occurred after colonization with P. aeruginosa. All colonized patients did not develop BPI-ANCA. The BPI-ANCA levels were fairly stable during the disease course, but decreased significantly following lung transplantation.

Conclusion: BPI-ANCA responses follow colonization with P. aeruginosa and may be predictive for lung damage.

Publication types

  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Antibodies, Antineutrophil Cytoplasmic / immunology*
  • Antimicrobial Cationic Peptides / immunology*
  • Biomarkers
  • Blood Proteins / immunology*
  • Carrier State / immunology
  • Carrier State / microbiology*
  • Child
  • Child, Preschool
  • Cross-Sectional Studies
  • Cystic Fibrosis / immunology
  • Cystic Fibrosis / microbiology*
  • Enzyme-Linked Immunosorbent Assay
  • Female
  • Forced Expiratory Volume
  • Humans
  • Infant
  • Male
  • Membrane Proteins / immunology*
  • Middle Aged
  • Prognosis
  • Pseudomonas aeruginosa / immunology*

Substances

  • Antibodies, Antineutrophil Cytoplasmic
  • Antimicrobial Cationic Peptides
  • Biomarkers
  • Blood Proteins
  • Membrane Proteins
  • bactericidal permeability increasing protein