Topical application of isosorbide dinitrate in patients with persistent constipation after pull-through surgery for Hirschsprung's disease

Eur J Pediatr Surg. 2007 Feb;17(1):62-5. doi: 10.1055/s-2007-964885.

Abstract

Aims: The aim of this study was to evaluate the anal manometric changes and the clinical effects after topical application of isosorbide dinitrate (ISDN) in patients with persistent constipation after pull-through surgery for Hirschsprung's disease (HD).

Methods: We studied 3 children (2 males and 1 female), aged 2, 3 and 5 years respectively, who had undergone the Soave-Boley surgical procedure for HD and who suffered from persistent constipation after operation. We performed a pre- and postoperative anorectal manometry study and we applied ISDN paste (1 mg/kg two times daily) in the anal region for three weeks. All patients were followed-up and re-evaluated at 1, 3, and 6 months.

Results: All patients showed an improvement of symptoms, with an average of 4 spontaneous evacuations per week. Prior to the topical treatment, the medium pressure was 115.6 mmHg (range 102 - 130 mmHg), the maximum pressure was 160 mmHg (range 145 - 175 mmHg), and the medium length of the high pressure zone was 1.8 cm (range 1.5 - 2.0 cm). At the 6 month follow-up, the medium pressure was 57.3 mmHg (range 52 - 61 mmHg, a decrease of 54.4 %), the maximum pressure was 98 mmHg (range 88 - 107 mmHg; a decrease of 38.7 %), and the medium length of the high pressure zone was 1.6 cm (range 1.4 - 1.8 cm; a decrease of 11.1 %).

Conclusions: Topical treatment with ISDN is a valid therapeutic alternative to an anal myotomy in patients with persistent constipation after pull-through surgery for HD. However, a greater number of cases and a longer follow-up are necessary to confirm the validity of our experience.

Publication types

  • Case Reports

MeSH terms

  • Administration, Topical
  • Anal Canal / drug effects
  • Anal Canal / physiopathology
  • Child, Preschool
  • Constipation / etiology*
  • Female
  • Hirschsprung Disease / complications
  • Hirschsprung Disease / surgery*
  • Humans
  • Isosorbide Dinitrate / administration & dosage
  • Isosorbide Dinitrate / therapeutic use*
  • Male
  • Manometry
  • Muscle Hypertonia / complications
  • Muscle Hypertonia / drug therapy*
  • Vasodilator Agents / administration & dosage
  • Vasodilator Agents / therapeutic use*

Substances

  • Vasodilator Agents
  • Isosorbide Dinitrate