A case of vanishing bile duct syndrome and IBD secondary to Hodgkin's lymphoma

Nat Clin Pract Gastroenterol Hepatol. 2008 Jan;5(1):49-53. doi: 10.1038/ncpgasthep1001.

Abstract

Background: A 39-year-old man presented with a 2-month history of abdominal pain, jaundice, non-bloody diarrhea, weakness, and weight loss. Initial evaluation revealed intrahepatic ductopenia consistent with vanishing bile duct syndrome and IBD, type unclassified. Although treatment with budesonide improved his symptoms, they worsened several months later. On repeat evaluation, he was found to have extensive lymphadenopathy and an elevated white blood cell count.

Investigations: Physical examination, laboratory investigations, abdominal ultrasound, CT scans, magnetic resonance cholangiopancreatography, endoscopic retrograde cholangiopancreatography, colonoscopies with biopsies, hepatic biopsy, axillary lymph node biopsy.

Diagnosis: Hodgkin's lymphoma with secondary vanishing bile duct syndrome and IBD, type unclassified.

Management: The initial symptoms were managed with budesonide, but following recurrence, the patient's underlying lymphoma was treated with nitrogen mustard and dexamethasone.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Bile Duct Diseases / diagnosis
  • Bile Duct Diseases / etiology*
  • Bile Duct Diseases / therapy
  • Hodgkin Disease / complications*
  • Hodgkin Disease / diagnosis
  • Hodgkin Disease / therapy
  • Humans
  • Inflammatory Bowel Diseases / diagnosis
  • Inflammatory Bowel Diseases / etiology*
  • Inflammatory Bowel Diseases / therapy
  • Male
  • Syndrome