Polymorphisms in genes related to folate and cobalamin metabolism and the associations with complex birth defects

Prenat Diagn. 2008 Jun;28(6):485-93. doi: 10.1002/pd.2006.

Abstract

Objective: To investigate the associations between biomarkers and genetic variants involved in homocysteine metabolism and the risk of complex birth defects.

Methods: Total homocysteine (tHcy), folate, cobalamin, apo-transcobalamin (apo-TC) and apo-haptocorrin (apo-HC) were measured in the amniotic fluid of 82 women who were pregnant with a child having a complex birth defect, such as neural tube defect, cleft lip and/or palate, heart defect or omphalocele, and in 110 women pregnant with a non-malformed child. The determined genotypes of the child comprised of 5, 10-methylenetetrahydrofolate reductase (MTHFR 677C > T, 1298A > C), methionine synthase (MTR 2756A > G), methionine synthase reductase (MTRR 66A > G) and transcobalamin (TCN2 776C > G). Univariate and multivariate logistic regression analyses were performed.

Results: Significantly lower cobalamin and higher apo-TC, apo-HC, tHcy and folate concentrations were determined in amniotic fluids of cases compared with controls (p< or =0.001). Logistic regression analysis revealed that after adjustment for maternal age, children carrying the MTHFR 677T allele showed a four-fold increased risk of having a complex birth defect, OR (95% CI) = 4.0 (1.1-15.4). Other genotypes did not show significant associations.

Conclusion: The MTHFR 677C > T polymorphism in conjunction with reduced folate- and/or cobalamin status may increase the risk of complex birth defects.

MeSH terms

  • 5-Methyltetrahydrofolate-Homocysteine S-Methyltransferase / genetics
  • Adult
  • Amniotic Fluid / chemistry
  • Case-Control Studies
  • Child
  • Congenital Abnormalities / genetics*
  • Female
  • Ferredoxin-NADP Reductase / genetics
  • Folic Acid / analysis
  • Folic Acid / genetics*
  • Folic Acid / metabolism
  • Genetic Predisposition to Disease
  • Genotype
  • Homocysteine / genetics
  • Homocysteine / metabolism
  • Humans
  • Methylenetetrahydrofolate Reductase (NADPH2) / genetics*
  • Polymorphism, Genetic
  • Pregnancy
  • Risk Factors
  • Transcobalamins / analysis
  • Transcobalamins / genetics
  • Vitamin B 12 / analysis
  • Vitamin B 12 / genetics*
  • Vitamin B 12 / metabolism

Substances

  • Transcobalamins
  • Homocysteine
  • Folic Acid
  • methionine synthase reductase
  • Ferredoxin-NADP Reductase
  • Methylenetetrahydrofolate Reductase (NADPH2)
  • 5-Methyltetrahydrofolate-Homocysteine S-Methyltransferase
  • Vitamin B 12