[Lung diseases associated with inherited disorders of surfactant metabolism]

Arch Pediatr. 2008 Oct;15(10):1560-7. doi: 10.1016/j.arcped.2008.07.016. Epub 2008 Sep 19.
[Article in French]

Abstract

Lung diseases associated with surfactant-metabolism disorders are a heterogeneous group of rare diseases. Intra-alveolar accumulation of protein related to surfactant dysfunction leads to cough, hypoxemia, and radiological-diffuse infiltration. Inherited deficiency of pulmonary surfactant protein B (SP-B) was initially described in infants who develop respiratory failure at birth. More recently, mutations in other constitutive surfactant proteins, such as surfactant protein C or implied in its metabolism, such as ATP-binding cassette, subfamily A, member 3 (ABCA3) and thyroid transcription factor 1 (TTF-1) were identified in newborns with respiratory distress as well as in children with chronic-infiltrative pneumonia. The aim of this review is therefore to summarize the current state of our knowledge in this area.

MeSH terms

  • ATP-Binding Cassette Transporters / genetics*
  • Child
  • DNA-Binding Proteins / genetics*
  • Humans
  • Lung Diseases / genetics*
  • Lung Diseases / metabolism
  • Pulmonary Surfactant-Associated Proteins / deficiency*
  • Pulmonary Surfactant-Associated Proteins / genetics*
  • Transcription Factors

Substances

  • ABCA3 protein, human
  • ATP-Binding Cassette Transporters
  • DNA-Binding Proteins
  • Pulmonary Surfactant-Associated Proteins
  • TTF1 protein, human
  • Transcription Factors