Sweet-like dermatosis in 2 patients with clinical features of dermatomyositis and underlying autoimmune disease

Arch Dermatol. 2008 Nov;144(11):1486-90. doi: 10.1001/archderm.144.11.1486.

Abstract

Background: The neutrophilic dermatoses comprise a group of cutaneous disorders that are characterized histopathologically by infiltration of the dermis with mature neutrophils with or without vessel wall destruction. Neutrophilic dermatoses have been reported in association with a variety of autoimmune diseases, most recently as a manifestation of lupus erythematosus.

Observations: We describe 2 patients with photodistributed violaceous plaques: one with associated heliotrope rash and malar erythema, and the other with scalp involvement and Gottron-like papules. In each case, the biopsy specimen revealed changes compatible with a neutrophilic dermatosis as opposed to an interface dermatitis. The first patient also had a history of Graves disease and primary biliary cirrhosis, while second patient had Wegener granulomatosis. The 2 patients responded to therapy with oral dapsone and prednisone, respectively.

Conclusions: The atypical presentation of neutrophilic dermatosis in 2 patients with clinical features of dermatomyositis and intercurrent autoimmune-mediated illnesses may suggest an expansion in the clinical spectrum of parainflammatory neutrophilic dermatoses. The finding of a neutrophilic dermatosis in a biopsy specimen from a patient without a classic clinical presentation should invoke a thoughtful search for underlying immune complex-mediated systemic disease.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Autoimmune Diseases / diagnosis*
  • Autoimmune Diseases / immunology
  • Biopsy, Needle
  • Dapsone / therapeutic use
  • Dermatomyositis / drug therapy
  • Dermatomyositis / immunology
  • Dermatomyositis / pathology*
  • Female
  • Follow-Up Studies
  • Granulomatosis with Polyangiitis / diagnosis
  • Granulomatosis with Polyangiitis / immunology
  • Graves Disease / diagnosis
  • Graves Disease / immunology
  • Humans
  • Immunohistochemistry
  • Middle Aged
  • Recurrence
  • Risk Assessment
  • Severity of Illness Index
  • Sweet Syndrome / drug therapy
  • Sweet Syndrome / immunology
  • Sweet Syndrome / pathology*
  • Treatment Outcome

Substances

  • Dapsone