Layer-specific genes reveal a rudimentary laminar pattern in human nodular heterotopia

Neurology. 2009 Sep 8;73(10):746-53. doi: 10.1212/WNL.0b013e3181af3397. Epub 2009 Jun 17.

Abstract

Objective: To define distinctive features of nodular heterotopia in specimens derived from drug-resistant patients with epilepsy by evaluating mRNA expression of three different layer-specific markers: Rorbeta, Er81, and Nurr1.

Methods: We analyzed the expression profile of these genes, recognized as markers mainly expressed in layer IV for Rorbeta, in layer V for Er81, and in layer VI for Nurr1, in surgical samples from 14 epileptic patients, using in situ hybridization. Six patients had subcortical nodular heterotopia and 8 patients were controls. The intrinsic organization of nodular formations and of the overlaying neocortex was assessed.

Results: In all patients, the 3 selected genes showed high cortical laminar specificity. In subcortical nodular heterotopia, the different gene expression profiles revealed a rudimentary laminar organization of the nodules. In the overlaying cortex, fewer cells expressed the 3 genes in the appropriate specific layer as compared to controls.

Conclusions: These data provide new insights into possible ontogenetic mechanisms of nodular heterotopia formation and show the potential role of layer-specific markers to elucidate the neuropathology of malformations of cortical development.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Cerebral Cortex / abnormalities*
  • Cerebral Cortex / pathology*
  • Cerebral Cortex / physiology
  • Child
  • DNA-Binding Proteins / biosynthesis
  • DNA-Binding Proteins / genetics
  • Female
  • Gene Expression Profiling / methods
  • Genetic Markers / genetics
  • Humans
  • Male
  • Malformations of Cortical Development / genetics
  • Malformations of Cortical Development / pathology
  • Nuclear Receptor Subfamily 1, Group F, Member 2
  • Nuclear Receptor Subfamily 4, Group A, Member 2
  • Periventricular Nodular Heterotopia / genetics*
  • Periventricular Nodular Heterotopia / pathology*
  • Receptors, Cytoplasmic and Nuclear / biosynthesis
  • Receptors, Cytoplasmic and Nuclear / genetics
  • Transcription Factors / biosynthesis
  • Transcription Factors / genetics
  • Young Adult

Substances

  • DNA-Binding Proteins
  • ETV1 protein, human
  • Genetic Markers
  • NR4A2 protein, human
  • Nuclear Receptor Subfamily 1, Group F, Member 2
  • Nuclear Receptor Subfamily 4, Group A, Member 2
  • RORB protein, human
  • Receptors, Cytoplasmic and Nuclear
  • Transcription Factors