FKBP12 is a critical regulator of the heart rhythm and the cardiac voltage-gated sodium current in mice

Circ Res. 2011 Apr 29;108(9):1042-52. doi: 10.1161/CIRCRESAHA.110.237867. Epub 2011 Mar 3.

Abstract

Rationale: FK506 binding protein (FKBP)12 is a known cis-trans peptidyl prolyl isomerase and highly expressed in the heart. Its role in regulating postnatal cardiac function remains largely unknown.

Methods and results: We generated FKBP12 overexpressing transgenic (αMyHC-FKBP12) mice and cardiomyocyte-restricted FKBP12 conditional knockout (FKBP12(f/f)/αMyHC-Cre) mice and analyzed their cardiac electrophysiology in vivo and in vitro. A high incidence (38%) of sudden death was found in αMyHC-FKBP12 mice. Surface and ambulatory ECGs documented cardiac conduction defects, which were further confirmed by electric measurements and optical mapping in Langendorff-perfused hearts. αMyHC-FKBP12 hearts had slower action potential upstrokes and longer action potential durations. Whole-cell patch-clamp analyses demonstrated an ≈ 80% reduction in peak density of the tetrodotoxin-resistant, voltage-gated sodium current I(Na) in αMyHC-FKBP12 ventricular cardiomyocytes, a slower recovery of I(Na) from inactivation, shifts of steady-state activation and inactivation curves of I(Na) to more depolarized potentials, and augmentation of late I(Na), suggesting that the arrhythmogenic phenotype of αMyHC-FKBP12 mice is attributable to abnormal I(Na). Ventricular cardiomyocytes isolated from FKBP12(f/f)/αMyHC-Cre hearts showed faster action potential upstrokes and a more than 2-fold increase in peak I(Na) density. Dialysis of exogenous recombinant FKBP12 protein into FKBP12-deficient cardiomyocytes promptly recapitulated alterations in I(Na) seen in αMyHC-FKBP12 myocytes.

Conclusions: FKBP12 is a critical regulator of I(Na) and is important for cardiac arrhythmogenic physiology. FKPB12-mediated dysregulation of I(Na) may underlie clinical arrhythmias associated with FK506 administration.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Action Potentials / physiology
  • Animals
  • Arrhythmias, Cardiac / genetics
  • Arrhythmias, Cardiac / physiopathology*
  • Calcium / metabolism
  • Calcium Channels, L-Type / physiology
  • Heart Conduction System / physiology*
  • In Vitro Techniques
  • Integrases / genetics
  • Long QT Syndrome / genetics
  • Long QT Syndrome / physiopathology
  • Mice
  • Mice, Knockout
  • Myocardial Contraction / physiology
  • Myocytes, Cardiac / physiology
  • Patch-Clamp Techniques
  • Potassium Channels / physiology
  • Sodium Channels / physiology*
  • Tacrolimus Binding Protein 1A / genetics*
  • Tacrolimus Binding Protein 1A / metabolism*

Substances

  • Calcium Channels, L-Type
  • Potassium Channels
  • Sodium Channels
  • Cre recombinase
  • Integrases
  • Tacrolimus Binding Protein 1A
  • Calcium