Preadipocyte factor-1 levels are higher in women with hypothalamic amenorrhea and are associated with bone mineral content and bone mineral density through a mechanism independent of leptin

J Clin Endocrinol Metab. 2011 Oct;96(10):E1634-9. doi: 10.1210/jc.2011-0600. Epub 2011 Jul 27.

Abstract

Context: Preadipocyte factor 1 (pref-1) is increased in anorexia nervosa and is associated negatively with bone mineral density (BMD). No previous studies exist on pref-1 in women with exercise-induced hypothalamic amenorrhea (HA), which similar to anorexia nervosa, is an energy-deficiency state associated with hypoleptinemia.

Objective: Our objective was to evaluate whether pref-1 levels are also elevated and associated with low BMD and to assess whether leptin regulates pref-1 levels in women with HA.

Design: Study 1 was a double-blinded, placebo-controlled randomized clinical trial of metreleptin administration in women with HA. Study 2 was an open-label study of metreleptin administration in low physiological, supraphysiological, and pharmacological doses in healthy women volunteers.

Setting and patients: At Beth Israel Deaconess Medical Center, 20 women with HA and leptin levels higher than 5 ng/ml and nine healthy control women participated in study 1, and five healthy women participated in study 2.

Intervention: For study 1, 20 HA subjects were randomized to receive either 0.08 mg/kg metreleptin (n = 11) or placebo (n = 9). For study 2, five healthy subjects received 0.01, 0.1, and 0.3 mg/kg metreleptin in both fed and fasting conditions for 1 and 3 d, respectively.

Main outcome measures: Circulating pref-1 and leptin levels were measured.

Results: Pref-1 was significantly higher in HA subjects vs. controls (P = 0.035) and negatively associated with BMD (ρ = -0.38; P < 0.01) and bone mineral content (ρ = -0.32; P < 0.05). Metreleptin administration did not alter pref-1 levels in any study reported herein.

Conclusions: Pref-1 is higher in HA subjects than controls. Metreleptin administration at low physiological, supraphysiological, and pharmacological doses does not affect pref-1 levels, suggesting that hypoleptinemia is not responsible for higher pref-1 levels and that leptin does not regulate pref-1.

Publication types

  • Randomized Controlled Trial
  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Amenorrhea / blood*
  • Amenorrhea / drug therapy
  • Body Composition / physiology
  • Body Mass Index
  • Body Weight / physiology
  • Bone Density / drug effects
  • Bone Density / physiology*
  • Calcium-Binding Proteins
  • Cross-Sectional Studies
  • Dose-Response Relationship, Drug
  • Double-Blind Method
  • Energy Metabolism / physiology
  • Estradiol / blood
  • Exercise / physiology
  • Female
  • Humans
  • Hypothalamic Diseases / blood*
  • Hypothalamic Diseases / drug therapy
  • Insulin-Like Growth Factor Binding Protein 3 / metabolism
  • Insulin-Like Growth Factor I / metabolism
  • Intercellular Signaling Peptides and Proteins / blood*
  • Leptin / analogs & derivatives
  • Leptin / deficiency
  • Leptin / pharmacology
  • Leptin / physiology*
  • Leptin / therapeutic use
  • Membrane Proteins / blood*
  • Young Adult

Substances

  • Calcium-Binding Proteins
  • DLK1 protein, human
  • Insulin-Like Growth Factor Binding Protein 3
  • Intercellular Signaling Peptides and Proteins
  • Leptin
  • Membrane Proteins
  • Estradiol
  • Insulin-Like Growth Factor I
  • metreleptin