Severe chronic diarrhea and maculopapular rash: a case report

World J Gastroenterol. 2011 Sep 14;17(34):3948-52. doi: 10.3748/wjg.v17.i34.3948.

Abstract

Systemic mastocytosis (SM) is a heterogeneous disease of the bone marrow characterized by abnormal growth, accumulation and activation of clonal mast cells (MCs). We report a case of SM with multi-organ involvement. A 30-year-old man presented with diarrhea, flushing, maculopapular rash with itching and weight loss. The upper and lower gastrointestinal endoscopies showed macroscopic involvement of stomach and duodenum; mucosal samples from stomach, duodenum, colon and distal ileum showed mucosal infiltration by large, spindle-shaped MCs with abnormal surface molecule expression (CD2 and CD25), a picture fully consistent with SM, according to the World Health Organization diagnostic criteria. A computed tomography scan showed diffuse lymphadenopathy, hepatosplenomegaly and diffuse small bowel involvement. Bone marrow aspirate and biopsy were diagnostic for SM; serum tryptase levels were increased (209 ng/mL, normal values < 20 ng/mL). The conclusive diagnosis was smouldering SM. There were no therapeutic indications except for treatment of symptoms. The patient was strictly followed up because of the risk of aggressive evolution.

Keywords: Bone marrow; Mast cells; Systemic mastocytosis; Tryptase.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Chronic Disease
  • Diarrhea / etiology*
  • Exanthema / etiology*
  • Exanthema / pathology*
  • Humans
  • Male
  • Mastocytosis, Systemic / complications*
  • Mastocytosis, Systemic / diagnosis*
  • Mastocytosis, Systemic / pathology