Spontaneous resolution of a Chiari malformation Type I and syrinx after supratentorial craniotomy for excision of a cavernous malformation

J Neurosurg. 2012 May;116(5):1054-9. doi: 10.3171/2012.1.JNS11580. Epub 2012 Feb 10.

Abstract

The pathogenesis of Chiari malformation Type I (CM-I) and associated syringomyelia is incompletely understood. Patients often present in middle age with incidental or minimally symptomatic CM-I, whose management is controversial. One option is clinical and radiographic observation of asymptomatic and minimally symptomatic patients. The authors here present the case of a 36-year-old woman who had been monitored for 6 years for a minimally symptomatic CM-I and cervicothoracic syrinx. After 5 years of follow-up, she suffered spontaneous rupture of a cerebral cavernous malformation when she was 27 weeks pregnant. The ruptured cavernous malformation and hematoma were operatively managed via a right frontal craniotomy. Ten months after the craniotomy for resection of the ruptured cavernous malformation, follow-up MRI demonstrated resolution of the CM-I and syrinx. Few similar cases have been reported in adults. This case argues for the presence of dynamic factors in the development and maintenance of CM-I and supports the nonoperative treatment of asymptomatic and minimally symptomatic patients.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Anesthesia, Epidural
  • Arnold-Chiari Malformation / surgery*
  • Brain Mapping
  • Cerebellum / pathology
  • Cesarean Section
  • Craniotomy*
  • Diplopia / etiology
  • Facial Paralysis / etiology
  • Female
  • Humans
  • Intracranial Arteriovenous Malformations / surgery*
  • Magnetic Resonance Imaging
  • Neurosurgical Procedures*
  • Postoperative Complications / therapy
  • Postoperative Period
  • Pregnancy
  • Rupture, Spontaneous
  • Syringomyelia / pathology
  • Syringomyelia / surgery*