Pediatric patients with common variable immunodeficiency: long-term follow-up

J Investig Allergol Clin Immunol. 2012;22(3):208-14.

Abstract

Background: Common variable immunodeficiency (CVID) is the most common form of symptomatic primary immunodeficiency disease. It is characterized by hypogammaglobulinemia, increased predisposition to infections, autoimmunity, and cancer.

Objectives: This study was performed to evaluate the clinical and immunological features of a group of pediatric patients with CVID.

Methods: The study population comprised 69 individuals with CVID diagnosed during childhood.

Results: The patients were followed up for a mean (SD) period of 5.2 (4.3) years. The mean diagnostic delay was 4.4 (3.6) years, which was significantly lower in patients who were diagnosed recently. Children were classified according to 5 clinical phenotypes: infections only (n=39), polyclonal lymphocytic infiltration (n=17), autoimmunity (n=12), malignancy (n=7), and enteropathy (n=3). Postdiagnosis survival (10-year) was 71%.

Conclusions: The high percentages of pediatric patients with CVID in Iran may be due to the considerable prevalence of parental consanguinity in the region and an underlying genetic background.

MeSH terms

  • Adolescent
  • Agammaglobulinemia / blood
  • Agammaglobulinemia / genetics
  • Agammaglobulinemia / immunology*
  • Agammaglobulinemia / mortality
  • Child
  • Child, Preschool
  • Common Variable Immunodeficiency / blood
  • Common Variable Immunodeficiency / genetics
  • Common Variable Immunodeficiency / immunology*
  • Common Variable Immunodeficiency / mortality
  • Delayed Diagnosis
  • Female
  • Follow-Up Studies
  • Genetic Predisposition to Disease
  • Humans
  • Immunoglobulins / blood
  • Iran / epidemiology
  • Male
  • Phenotype

Substances

  • Immunoglobulins