Encapsulating peritoneal sclerosis in children on chronic PD: a survey from the European Paediatric Dialysis Working Group

Nephrol Dial Transplant. 2013 Jul;28(7):1908-14. doi: 10.1093/ndt/gfs603. Epub 2013 Jan 24.

Abstract

Background: Encapsulating peritoneal sclerosis (EPS) is a rare complication of peritoneal dialysis (PD) that is associated with significant morbidity and mortality in adults. There are scarce data for children. We performed a 10-year survey to determine the prevalence, risk factors and outcome for EPS in children.

Methods: Chronic PD patients in 14 dialysis units participating in the European Paediatric Dialysis Working Group between January 2001 and December 2010 were included in this study.

Results: Twenty-two cases of EPS were reported (prevalence 1.5%; 8.7 per 1000 patient-years on PD). Median PD vintage was 5.9 (1.6-10.2) in EPS and 1.7 (0.7-7.7) years in the remainder of the PD population (P<0.0001). EPS patients had a significantly higher peritonitis rate than non-EPS patients (P=0.2). EPS was diagnosed while the child was on PD in 17 (77%), after conversion to haemodialysis (HD) in 3 and after transplantation in 2. Fifteen of 17 (88%) developed ultrafiltration (UF) failure. The median interval between UF failure and presentation with bowel obstruction was 2.8 (0.02-5.8) months. Twenty (91%) had clinical and radiological signs of bowel obstruction. Enterolysis was performed in 14 and 19 received immunosuppression or tamoxifen. Nine required parenteral nutrition. At final follow-up 4.8 (1.3-8.7) years after EPS diagnosis, 3 patients died, 11 had a functioning transplant and 8 were on HD.

Conclusions: The prevalence of EPS in European children on PD is comparable with that of adult PD patients, but mortality from paediatric EPS is significantly lower. A high index of suspicion is required for the diagnosis of EPS in children with longer dialysis duration, a high peritonitis rate and UF failure.

Keywords: UF failure; encapsulating peritoneal sclerosis, paediatrics, peritoneal dialysis; peritonitis.

Publication types

  • Multicenter Study

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • Europe
  • Female
  • Follow-Up Studies
  • Health Surveys
  • Humans
  • Kidney Failure, Chronic / complications*
  • Male
  • Peritoneal Dialysis / adverse effects*
  • Peritoneal Dialysis / mortality
  • Peritoneal Fibrosis / diagnosis
  • Peritoneal Fibrosis / etiology*
  • Peritoneal Fibrosis / mortality
  • Peritoneal Fibrosis / therapy
  • Peritonitis / etiology*
  • Peritonitis / pathology
  • Prognosis
  • Risk Factors
  • Survival Rate
  • Ultrafiltration
  • Young Adult