Incomplete penetrance of the C9ORF72 hexanucleotide repeat expansions: frequency in a cohort of geriatric non-demented subjects

J Alzheimers Dis. 2014;39(1):19-22. doi: 10.3233/JAD-131172.

Abstract

We genotyped for the C9ORF72 hexanucleotide repeat expansion a population of 156 non-demented elderly subjects, recruited in a geriatric unit as control group for association studies in patients with Alzheimer's disease (AD), and found two carriers (1.2%). The first was referred for subjective memory complaints, at age 81. He was followed up until age 84 and did not develop dementia. The second was an 80-year old volunteer (spouse and caregiver of a patient with AD), non-demented at time of recruitment. We have not had information on her condition since that time. These results suggest that the penetrance of the mutation is definitely incomplete.

Keywords: C9ORF72 hexanucleotide repeat expansion; dementia; elderly; frontotemporal lobar degeneration; penetrance.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Aged, 80 and over
  • Alzheimer Disease / genetics
  • C9orf72 Protein
  • Cohort Studies
  • DNA Repeat Expansion*
  • Female
  • Genotype
  • Geriatric Assessment / statistics & numerical data*
  • Heterozygote
  • Humans
  • Male
  • Middle Aged
  • Penetrance
  • Proteins / genetics*

Substances

  • C9orf72 Protein
  • C9orf72 protein, human
  • Proteins