Unexpected high frequency of skeletal dysplasia in idiopathic short stature and small for gestational age patients

Eur J Endocrinol. 2014 Apr 10;170(5):677-84. doi: 10.1530/EJE-13-0864. Print 2014 May.

Abstract

Objective: To assess the prevalence of skeletal dysplasias (SDs) in patients with idiopathic short stature (ISS) or small for gestational age (SGA) status.

Setting: Rare Endocrine/Growth Diseases Center in Paris, France.

Design: A prospective study on consecutive patients with ISS and SGA enrolled from 2004 to 2009.

Method: We used a standardized workup to classify patients into well-established diagnostic categories. Of 713 patients with ISS (n=417) or SGA status (n=296), 50.9% underwent a skeletal survey. We chose patients labeled normal or with a prepubertal slowdown of growth as a comparison group.

Results: Diagnoses were ISS (16.9%), SGA (13.5%), normal growth (24.5%), transient growth rate slowing (17.3%), endocrine dysfunction (12%), genetic syndrome (8.9%), chronic disease (5.1%), and known SD (1.8%). SD was found in 20.9% of SGA and 21.8% ISS patients and in only 13.2% in our comparison group. SD prevalence was significantly higher in the ISS group than in the comparison group, especially (50%) for patients having at least one parent whose height was <-2 SDS. Dyschondrosteosis and hypochondroplasia were the most frequently identified SD, and genetic anomaly was found in 61.5 and 30% respectively. Subtle SD was found equally in the three groups and require long-term growth follow-up to evaluate the impact on final height.

Conclusion: SD may explain more than 20% of cases of growth retardation ascribed to ISS or SGA, and this proportion is higher when parental height is <-2 SDS. A skeletal survey should be obtained in patients with delayed growth in a context of ISS or SGA.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Bone Diseases, Developmental / epidemiology
  • Bone Diseases, Developmental / genetics
  • Bone Diseases, Developmental / physiopathology*
  • Bone and Bones / abnormalities
  • Bone and Bones / physiopathology
  • Child
  • Child, Preschool
  • Cohort Studies
  • Dwarfism / epidemiology
  • Dwarfism / genetics
  • Dwarfism / physiopathology
  • Family Health
  • Female
  • Fetal Growth Retardation / epidemiology
  • Fetal Growth Retardation / genetics
  • Fetal Growth Retardation / physiopathology*
  • France / epidemiology
  • Genetic Variation
  • Growth Disorders / epidemiology
  • Growth Disorders / etiology*
  • Growth Disorders / genetics
  • Growth Disorders / physiopathology
  • Hospitals, Pediatric
  • Hospitals, Teaching
  • Humans
  • Infant
  • Infant, Small for Gestational Age
  • Limb Deformities, Congenital / epidemiology
  • Limb Deformities, Congenital / genetics
  • Limb Deformities, Congenital / physiopathology
  • Lordosis / epidemiology
  • Lordosis / genetics
  • Lordosis / physiopathology
  • Male
  • Osteochondrodysplasias / epidemiology
  • Osteochondrodysplasias / genetics
  • Osteochondrodysplasias / physiopathology
  • Prevalence
  • Prospective Studies
  • Referral and Consultation

Supplementary concepts

  • Hypochondroplasia
  • Leri-Weil syndrome