Identification of a GJA3 mutation in a Chinese family with congenital nuclear cataract using exome sequencing

Indian J Biochem Biophys. 2013 Aug;50(4):253-8.

Abstract

Congenital cataract, a clinically and genetically heterogeneous lens disorder is defined as any opacity of the lens presented from birth and is responsible for approximately 10% of worldwide childhood poor vision or blindness. To identify the genetic defect responsible for congenital nuclear cataract in a four-generation Chinese Han family, exome and direct Sanger sequencings were conducted and a missense variant c.139G>A (p.D47N) in the gap junction protein-alpha 3 gene (GJA3) was identified. The variant co-segregated with patients of the family and was not observed in unaffected family members or normal controls. The above findings indicated that the variant was a pathogenic mutation. The mutation p.D47N was found in the first extracellular loop (El) domain of GJA3 protein. Our data suggest that exome sequencing is a powerful tool to discover mutation(s) in cataract, a disorder with high genetic heterogeneity. Our findings may also provide new insights into the cause and diagnosis of congenital nuclear cataract and have implications for genetic counseling.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Animals
  • Asian People / genetics*
  • Base Sequence
  • Cataract / congenital*
  • Cataract / genetics*
  • Cattle
  • Connexins / genetics*
  • DNA Mutational Analysis*
  • Exome / genetics*
  • Female
  • Humans
  • Male
  • Middle Aged
  • Mutation
  • Pedigree*
  • Phenotype

Substances

  • Connexins
  • GJA3 protein, human