Thyroid-like low-grade nasopharyngeal papillary adenocarcinoma: case report and literature review

Pathol Res Pract. 2014 Dec;210(12):1142-5. doi: 10.1016/j.prp.2014.04.020. Epub 2014 May 9.

Abstract

Thyroid-like low-grade nasopharyngeal papillary adenocarcinoma (TL-LGNPPA) is an extremely rare neoplasm characterized by morphological analogy to papillary thyroid carcinoma and abnormal expression of thyroid transcription factor-1 (TTF-1). Here we report a novel case of TL-LGNPPA with literature review. The patient was a 43-year-old woman complaining of nasal obstruction. Laryngoscopic study and computed tomography identified a pedunculated mass located on the posterior edge of the left nasal septum. Histologically, the tumor consisted of papillary growth of cuboidal or columnar epithelium. Tubular architecture and a spindle cell component were also observed focally. Some tumor cells exhibited intra-nuclear cytoplasmic inclusions. Immunohistochemically, the neoplastic cells were positive for pancytokeratin (AE1/AE3), CK7, CK19, TTF-1, vimentin and HBME1, but negative for thyroglobulin, Pax8 and CK5/6. Ki67-labeling index reached 5% in the most concentrated spot. Despite the morphological and immunohistochemical similarity to papillary thyroid carcinoma, no BRAF V600E mutation was detected by mutation-specific immunohistochemistry. The patient had neither local recurrence nor distant metastasis 19 months after removal of the tumor.

Keywords: BRAF V600E; Immunohistochemistry; Low-grade papillary adenocarcinoma; Nasopharynx; Thyroid transcription factor-1.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adenocarcinoma, Papillary / diagnosis
  • Adenocarcinoma, Papillary / metabolism
  • Adenocarcinoma, Papillary / pathology*
  • Adult
  • Biomarkers, Tumor / metabolism*
  • Carcinoma / diagnosis
  • Carcinoma / metabolism
  • Carcinoma / pathology*
  • Carcinoma, Papillary
  • Female
  • Humans
  • Nasopharyngeal Carcinoma
  • Nasopharyngeal Neoplasms / diagnosis
  • Nasopharyngeal Neoplasms / metabolism
  • Nasopharyngeal Neoplasms / pathology*
  • Neoplasm Grading
  • Neoplasm Recurrence, Local / diagnosis
  • Neoplasm Recurrence, Local / genetics
  • Thyroid Cancer, Papillary
  • Thyroid Gland / pathology*
  • Thyroid Neoplasms / diagnosis
  • Thyroid Neoplasms / metabolism
  • Thyroid Neoplasms / pathology*

Substances

  • Biomarkers, Tumor