CDK5-mediated phosphorylation and autophagy of RKIP regulate neuronal death in Parkinson's disease

Neurobiol Aging. 2014 Dec;35(12):2870-2880. doi: 10.1016/j.neurobiolaging.2014.05.034. Epub 2014 Jun 11.

Abstract

Raf kinase inhibitor protein (RKIP) is a major negative mediator of the extracellular signal-related kinase (ERK)/mitogen-activated protein kinase (MAPK) pathway. The downregulation of RKIP is correlated with many cancers, but the mechanisms that underlie this downregulation and its roles in the nervous system remain unclear. Here, we demonstrate that RKIP is a substrate of cyclin-dependent kinase 5 (CDK5) in neurons and that the phosphorylation of RKIP at T42 causes the release of Raf-1. Moreover, T42 phosphorylation promotes the exposure and recognition of the target motif "KLYEQ" in the C-terminus of RKIP by chaperone Hsc70 and the subsequent degradation of RKIP via chaperone-mediated autophagy (CMA). Furthermore, in the brain sample of Parkinson's disease (PD) patients and in 1-methyl-4-phenyl-1,2,3,6-tetrahydropyridine hydrochloride-induced and transgenic PD models, we demonstrate that CDK5-mediated phosphorylation and autophagy of RKIP are involved in the overactivation of the ERK/MAPK cascade, leading to S-phase reentry and neuronal loss. These findings provide evidence for the role of the CDK5/RKIP/ERK pathway in PD pathogenesis and suggest that this pathway may be a suitable therapeutic target in PD.

Keywords: Chaperone-mediated autophagy; Cyclin-dependent kinase 5; Parkinson's disease; Protein phosphorylation; Raf kinase inhibitor protein.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Autophagy / genetics*
  • Cells, Cultured
  • Cyclin-Dependent Kinase 5 / physiology*
  • Disease Models, Animal
  • Humans
  • MAP Kinase Signaling System / physiology
  • Molecular Targeted Therapy
  • Neurons / pathology*
  • Parkinson Disease / genetics*
  • Parkinson Disease / pathology*
  • Parkinson Disease / therapy
  • Phosphatidylethanolamine Binding Protein / metabolism*
  • Phosphatidylethanolamine Binding Protein / physiology
  • Phosphorylation / genetics
  • Rats

Substances

  • Phosphatidylethanolamine Binding Protein
  • Cyclin-Dependent Kinase 5