A Phase I Study of Clofarabine With Multiagent Chemotherapy in Childhood High Risk Relapse of Acute Lymphoblastic Leukemia (VANDEVOL Study of the French SFCE Acute Leukemia Committee)

Pediatr Blood Cancer. 2016 Feb;63(2):270-5. doi: 10.1002/pbc.25751. Epub 2015 Sep 16.

Abstract

Background: Current outcome of very early relapse of acute lymphoblastic leukemia (ALL) in children remains poor. As a single agent, clofarabine provided a response rate of 26% in childhood ALL second relapse and, in combination with cyclophosphamide and etoposide, a 44% complete remission and complete remission without platelet recovery (CR+CRp) rate. Further multi-drug combinations need to be investigated. We used the VANDA regimen as a template, cytarabine being replaced by clofarabine.

Patients and methods: A phase I study combining escalating doses of clofarabine (25% increments from 20 to 40 mg/m(2)/d) with fixed doses of mitoxantrone, etoposide, asparaginase, and dexamethasone was undertaken in children presenting with very early or second or post-transplant ALL relapse.

Results: Twenty patients were enrolled, 19 were evaluable. Four patients had previously been allografted. Dose-limiting toxicity (DLT) appeared at dose level 3 (32 mg/m(2)), one out of six patients experienced a liver DLT. At dose level 4 (40 mg/m(2)), four DLT occurred (two fungal infection and two liver DLT). The maximum tolerated dose (MTD) of clofarabine was thus determined to be 32 mg/m(2). There was no toxic death. Eleven (57.9%) patients achieved a CR. Six patients proceeded to allogeneic stem cell transplantation.

Conclusion: Clofarabine MTD was 32 mg/m(2)/d in this combination which appeared feasible and effective in this population.

Keywords: acute lymphoblastic leukemia; child; clofarabine; phase I; resistant disease.

Publication types

  • Clinical Trial, Phase I
  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adenine Nucleotides / administration & dosage*
  • Adenine Nucleotides / adverse effects
  • Adolescent
  • Antineoplastic Combined Chemotherapy Protocols / administration & dosage*
  • Antineoplastic Combined Chemotherapy Protocols / adverse effects
  • Arabinonucleosides / administration & dosage*
  • Arabinonucleosides / adverse effects
  • Asparaginase / therapeutic use
  • Child
  • Child, Preschool
  • Clofarabine
  • Dexamethasone / therapeutic use
  • Dose-Response Relationship, Drug
  • Etoposide / therapeutic use
  • Female
  • Humans
  • Male
  • Maximum Tolerated Dose
  • Mitoxantrone / therapeutic use
  • Neoplasm Recurrence, Local / drug therapy*
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / drug therapy*
  • Salvage Therapy / methods
  • Young Adult

Substances

  • Adenine Nucleotides
  • Arabinonucleosides
  • Etoposide
  • Clofarabine
  • Dexamethasone
  • Mitoxantrone
  • Asparaginase