Enteric nervous system α-synuclein immunoreactivity in idiopathic REM sleep behavior disorder

Neurology. 2015 Nov 17;85(20):1761-8. doi: 10.1212/WNL.0000000000002126. Epub 2015 Oct 16.

Abstract

Objective: To investigate the expression of α-synuclein in colonic biopsies of patients with idiopathic REM sleep behavior disorder (iRBD) and address if α-synuclein immunostaining of tissue obtained via colonic biopsies holds promise as a diagnostic biomarker for prodromal Parkinson disease (PD).

Methods: Patients with iRBD, patients with PD, and healthy controls were prospectively recruited to undergo colonic biopsies for comparison of α-synuclein immunoreactivity patterns between the groups by using 2 different antibodies.

Results: There was no difference in colonic mucosal and submucosal immunostaining between groups using the 15G7 α-synuclein antibody, which was found in almost all participants enrolled in this study. By contrast, immunostaining for serine 129-phosphorylated α-synuclein (pSyn) in submucosal nerve fibers or ganglia was found in none of 14 controls but was observed in 4 of 17 participants with iRBD and 1 out of 19 patients with PD.

Conclusions: The present findings of pSyn immunostaining of colonic biopsies in a substantial proportion of iRBD participants raise the possibility that this tissue marker may be a suitable candidate to study further as a prodromal PD marker in at-risk cohorts.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Biomarkers / analysis
  • Colon / chemistry*
  • Colon / innervation
  • Colon / pathology
  • Enteric Nervous System / chemistry*
  • Enteric Nervous System / pathology
  • Female
  • Humans
  • Male
  • Middle Aged
  • Prospective Studies
  • REM Sleep Behavior Disorder / diagnosis*
  • REM Sleep Behavior Disorder / metabolism
  • Submucous Plexus / chemistry
  • Submucous Plexus / pathology
  • alpha-Synuclein / analysis*

Substances

  • Biomarkers
  • alpha-Synuclein