A case of maternal-foetal chimerism identified during routine histocompatibility testing for hematopoietic stem cell transplantation

Int J Immunogenet. 2016 Feb;43(1):1-7. doi: 10.1111/iji.12241. Epub 2015 Dec 12.

Abstract

This report describes a case of maternal-foetal chimerism identified in a boy diagnosed with SCID, who underwent HLA testing in preparation for HSCT. The first analysis was carried out on DNA from peripheral blood and included HLA-A, HLA-B, HLA-DRB1 typing using PCR-SSO. The patient's HLA-B typing results were noninterpretable. All samples were re-typed for HLA-B using PCR-SSP, again resulting in noninterpretable typing of patient's HLA-B. In both cases, several weak positive probes/reactions interfered with the interpretation when using commercial software. Next round of HLA typing, using PCR-SSP and PCR-SSO methods, included the patient's bone marrow sample and HLA-C locus, but interpretation was again not possible. The PCR-STR analysis performed on both peripheral blood and bone marrow samples revealed seven STRs for which two maternal and one paternal allele were detected. Retrospective manual interpretation of HLA-B and HLA-C typing revealed that weak positive reactions were indeed owed to paternal HLA-B and HLA-C alleles and that the patient had both maternal and one paternal allele. Retyping of HLA-B and HLA-C loci and STR analysis on the patient's buccal cells sample revealed the expected one maternal/one paternal allele pattern. In summary, the combination of several different typing methods and manual interpretation were necessary to obtain the patient's HLA typing results.

Publication types

  • Case Reports

MeSH terms

  • Alleles
  • Bone Marrow / immunology
  • Chimerism*
  • HLA-A Antigens / immunology
  • HLA-B Antigens / genetics
  • HLA-B Antigens / immunology
  • HLA-C Antigens / immunology
  • HLA-DRB1 Chains / immunology
  • Hematopoietic Stem Cell Transplantation*
  • Histocompatibility Testing
  • Histocompatibility, Maternal-Fetal / immunology*
  • Humans
  • Infant
  • Male

Substances

  • HLA-A Antigens
  • HLA-B Antigens
  • HLA-C Antigens
  • HLA-DRB1 Chains