Two Novel TEX15 Mutations in a Family with Nonobstructive Azoospermia

Gynecol Obstet Invest. 2017;82(3):283-286. doi: 10.1159/000468934. Epub 2017 Mar 30.

Abstract

Aim: Genetic investigations explain only a small percentage of cases of nonobstructive azoospermia (NOA), a condition that affects up to 2% of infertile couples. This study aimed to identify further genomic variants that are associated with primary spermatogenic failure within the testis.

Methods: One family with 2 infertile siblings affected by NOA was genotyped by whole-exome sequencing. DNA variants were filtered based on quality score, allele frequency, and functional roles of genes in spermatogenesis.

Results: Both NOA males were compound heterozygotes for a nonsense mutation and a single nucleotide deletion leading to premature stop codons in the TEX15 gene (c.2419A>T, p.Lys807*, and c.3040delT, p.Ser1014Leufs*5, respectively). The single mutations were identified only on one allele in 6 family members, including 3 fertile males who conceived naturally.

Conclusion: This is the second reported case of a TEX15 deleterious mutation cosegregating with NOA in a family in which the infertile phenotype is reminiscent of the one observed in the TEX15-knockout mouse, confirming that TEX15 plays a critical role in normal spermatogenesis and its defects may be responsible for a number of NOA cases.

Keywords: Infertility; Loss of function; Molecular diagnosis; Mutation; Nonobstructive azoospermia; Pedigree; Reproductive medicine; Spermatogenic failure; TEX15 gene; Whole-exome sequencing.

MeSH terms

  • Alleles
  • Animals
  • Azoospermia / genetics*
  • Cell Cycle Proteins / genetics*
  • Codon, Nonsense / genetics
  • Female
  • Gene Frequency
  • Genetic Predisposition to Disease
  • Humans
  • Male
  • Mice
  • Mutation*
  • Phenotype
  • Spermatogenesis / genetics
  • Testis

Substances

  • Cell Cycle Proteins
  • Codon, Nonsense
  • TEX15 protein, human

Supplementary concepts

  • Azoospermia, Nonobstructive