Use of liothyronine without levothyroxine in the treatment of mild consumptive hypothyroidism caused by hepatic hemangiomas

Endocr J. 2017 Jun 29;64(6):639-643. doi: 10.1507/endocrj.EJ16-0559. Epub 2017 Apr 18.

Abstract

There have been reports of the use of levothyroxine or levothyroxine plus liothyronine for consumptive hypothyroidism caused by hepatic hemangiomas. Administration of levothyroxine without liothyronine can be inadequate to maintain normal levels of both free T3 and free T4 in some patients. However, there is no report of treatment with liothyronine plus propranolol. We herein present a case in which we used liothyronine therapy for multifocal hepatic hemangiomas in a Japanese patient with low free T3 and normal free T4 levels. A 2-month-old Japanese male was referred to our hospital because of jaundice. Abdominal computed tomography showed multifocal hemangiomas in both lobes of the liver. TSH level was elevated, free T3 level was low, free T4 level was normal, and hypothyroidism due to hepatic hemangiomas was diagnosed. In addition to propranolol, liothyronine was started. We used liothyronine without levothyroxine for hypothyroidism because only free T3 level had decreased, whereas free T4 level remained in the normal range. The TSH and free T3 levels normalized in this patient in less than 1 month. The liothyronine dose was gradually reduced with regression of the hemangiomas, and liothyronine administration was discontinued at the age of 5 months. At the age of 11 months, growth and neurological development of the patient met age-specific norms, and he was euthyroid at that time. This is the first report demonstrating the use of liothyronine with propranolol for treatment of this type of consumptive hypothyroidism.

Keywords: Consumptive hypothyroidism; Hemangioma; Liothyronine; Type 3 deiodinase.

Publication types

  • Case Reports

MeSH terms

  • Hemangioma / diagnostic imaging
  • Hemangioma / drug therapy
  • Hemangioma / physiopathology*
  • Hormone Replacement Therapy*
  • Humans
  • Hypothyroidism / blood
  • Hypothyroidism / drug therapy*
  • Hypothyroidism / etiology
  • Hypothyroidism / physiopathology
  • Infant
  • Liver / diagnostic imaging
  • Liver / drug effects
  • Liver / physiopathology
  • Liver Neoplasms / diagnostic imaging
  • Liver Neoplasms / drug therapy
  • Liver Neoplasms / physiopathology*
  • Male
  • Propranolol / therapeutic use
  • Severity of Illness Index
  • Thyroid Gland / drug effects*
  • Thyroid Gland / physiopathology
  • Thyroxine / blood
  • Tomography, X-Ray Computed
  • Treatment Outcome
  • Triiodothyronine / blood
  • Triiodothyronine / therapeutic use*
  • Ultrasonography, Doppler
  • Vasodilator Agents / therapeutic use

Substances

  • Vasodilator Agents
  • Triiodothyronine
  • Propranolol
  • Thyroxine