Parkinson's disease associated with 22q11.2 deletion: Clinical characteristics and response to treatment

Rev Neurol (Paris). 2017 Jun;173(6):406-410. doi: 10.1016/j.neurol.2017.03.021. Epub 2017 Apr 29.

Abstract

Background: While it is known that 22q11.2 microdeletions (22q11.2-del) increase the risk of Parkinson's disease (PD), the characteristics of PD associated with 22q11.2-del have not been specifically explored.

Objective: This report aimed to assess the clinical characteristics and treatment responses of PD patients with 22q11.2-del, and to describe any features that might lead neurologists to investigate the comorbidity.

Methods: Nine PD patients (eight men, one woman) with 22q11.2-del were followed at seven centers of the French PD Expert Network (Ns-Park).

Results: PD diagnosis was made before 22q11.2-del diagnosis in seven cases; their main characteristics were early onset (32-48 years) and good initial levodopa sensitivity, but with a course characterized by severe and early-onset levodopa-induced motor complications and psychiatric manifestations. Three patients received deep brain stimulation (DBS) that was effective.

Conclusion: Searching for 22q11.2-del in PD patients presenting with suggestive features is relevant as the clinical presentation is similar to idiopathic PD, but with other associated characteristics, including a severe evolution. Results with DBS are similar to those reported for idiopathic PD.

Keywords: 22q11.2 deletion syndrome; Deep brain stimulation; Early-onset Parkinson's disease; Genetics; Phenotype.

MeSH terms

  • 22q11 Deletion Syndrome / complications*
  • 22q11 Deletion Syndrome / diagnosis
  • 22q11 Deletion Syndrome / therapy
  • Adult
  • Cohort Studies
  • Deep Brain Stimulation
  • Female
  • France
  • Humans
  • Levodopa / therapeutic use
  • Male
  • Middle Aged
  • Parkinson Disease / complications*
  • Parkinson Disease / diagnosis
  • Parkinson Disease / genetics
  • Parkinson Disease / therapy
  • Phenotype
  • Treatment Outcome

Substances

  • Levodopa