H3.1 K36M mutation in a congenital-onset soft tissue neoplasm

Pediatr Blood Cancer. 2017 Dec;64(12). doi: 10.1002/pbc.26633. Epub 2017 May 16.

Abstract

We describe a patient who presented with a congenital soft tissue lesion initially diagnosed as infantile fibromatosis at 15 days of age. Unusually, the mass demonstrated malignant progression leading to death at 20 months of age. Biological progression to malignancy is not known to occur in fibromatosis, and fibrosarcoma is not known to progress from a benign lesion. Whole-exome sequencing of the tumor identified a driver mutation in histone H3.1 at lysine (K)36. Our findings support the link between oncohistones and infantile soft tissue tumors and provide additional evidence for the oncogenic effects of p.K36M in H3 variants.

Keywords: histone H3.1; infantile cancer; posttranslational histone modification; soft tissue tumor.

Publication types

  • Case Reports

MeSH terms

  • Base Sequence
  • Exome / genetics*
  • Fibroma / congenital
  • Fibroma / genetics*
  • Fibroma / pathology
  • Histones / genetics*
  • Humans
  • Infant
  • Infant, Newborn
  • Mutation*
  • Pathology, Molecular
  • Soft Tissue Neoplasms / congenital*
  • Soft Tissue Neoplasms / genetics*
  • Soft Tissue Neoplasms / pathology

Substances

  • Histones