Geoepidemiology, clinical manifestations and outcome of primary biliary cholangitis in Greece

Eur J Intern Med. 2017 Jul:42:81-88. doi: 10.1016/j.ejim.2017.05.006. Epub 2017 May 20.

Abstract

Background & aims: Primary biliary cholangitis (PBC) is a disease with rising prevalence and considerable geographical variation. To describe the prevalence, spatial and time distribution, baseline characteristics, response to treatment, outcome and the validity of GLOBE score in a large cohort of Greek PBC patients as an independent validation of this score has not been done so far.

Methods: The last 16years, 482 PBC patients (86.5% females) were evaluated and analysed retrospectively, using a prospectively collected database. Special attention was paid to the assessment of treatment response according to GLOBE score.

Results: Age at initial evaluation was 56.3±13.7years. Among 432 Thessaly residents, prevalence was 582/million (non-homogeneous distribution). Nineteen districts showed a prevalence >800/million. Symptomatic disease onset could be identified in 91 patients, with a significant peak during spring (P=0.03). At diagnosis, 43.6% were asymptomatic and 16.2% cirrhotic. Male sex (P=0.02), older age (P<0.001), alcohol consumption (P<0.01) and concomitant liver disease (P<0.001) were negative prognostic factors for cirrhosis. During a median [interquartile range, range] follow-up of 5.1 (7.8, 15.7) years, 62 patients died or underwent liver transplantation. Patients with GLOBE score>0.30 had significantly worse prognosis (P<0.001) with 5-, 10-, and 15-year survival rates of 84%, 50% and 42%.

Conclusions: There is increased PBC prevalence in Thessaly with remarkable geographic clustering and seasonal variability. PBC is diagnosed at early stages although males had a more advanced disease. GLOBE score applies perfectly in Greek patients and this will likely help detecting patients that may benefit from new therapies.

Keywords: Autoantibodies; Geoepidemiology; Liver autoimmunity; Natural history; Primary biliary cholangitis; Primary biliary cirrhosis; Prognosis.

MeSH terms

  • Adult
  • Aged
  • Alcohol Drinking / epidemiology
  • Autoantibodies / blood
  • Carcinoma, Hepatocellular / epidemiology*
  • Cholangitis / complications*
  • Cholangitis / therapy
  • Female
  • Greece / epidemiology
  • Humans
  • Liver Cirrhosis, Biliary / epidemiology*
  • Liver Neoplasms / epidemiology*
  • Liver Transplantation
  • Logistic Models
  • Male
  • Middle Aged
  • Multivariate Analysis
  • Retrospective Studies
  • Risk Factors
  • Seasons
  • Survival Analysis
  • Treatment Outcome

Substances

  • Autoantibodies