Pivotal Role of Lesional and Perilesional T/B Lymphocytes in Pemphigus Pathogenesis

J Invest Dermatol. 2017 Nov;137(11):2362-2370. doi: 10.1016/j.jid.2017.05.032. Epub 2017 Jun 22.

Abstract

Pemphigus is a skin and mucosal membrane-targeting autoimmune bullous disease. Previous studies have shown that circulating anti-desmoglein1/3 antibodies are pathogenic and mediate blister formation. However, the role of infiltrating immune cells in lesional skin has not been fully investigated. In this study we showed that there existed a large number of B and T lymphocytes and plasma cells in the skin lesions by immunohistochemistry and immunofluorescence staining. In addition, a significantly increased number of Dsg1- and Dsg3-specific B cells could be identified by flow cytometric analysis or enzyme-linked immunospot technique (i.e., ELISPOT) assay. Furthermore, anti-Dsg1 and Dsg3 antibodies could be detected from the supernatant of in vitro cultures with isolated lymphocytes from lesional skin. We found that most T lymphocytes infiltrating pemphigus vulgaris lesions were CD4+ T helper cells expressing IL-21 and IL-17a but not typical T follicular helper cells expressing CXCR5. Additionally, our microarray assay showed that the level of chemokine CCL19 was significantly elevated, suggesting active T-/B-lymphocyte trafficking and aggregation in the pemphigus vulgaris lesions. Collectively, our results suggest a critical role of locally infiltrating lymphocytes in pemphigus pathogenesis.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • B-Lymphocytes / immunology*
  • B-Lymphocytes / metabolism
  • Biopsy, Needle
  • Blotting, Western
  • Case-Control Studies
  • Cell Movement / immunology
  • Desmoglein 1 / immunology
  • Desmoglein 1 / metabolism*
  • Enzyme-Linked Immunosorbent Assay / methods
  • Enzyme-Linked Immunospot Assay
  • Female
  • Humans
  • Immunohistochemistry
  • Interleukin-17 / metabolism
  • Interleukins / metabolism
  • Male
  • Pemphigus / immunology*
  • Pemphigus / pathology*
  • Reference Values
  • Role
  • T-Lymphocytes / immunology*
  • T-Lymphocytes / metabolism

Substances

  • Desmoglein 1
  • Interleukin-17
  • Interleukins
  • interleukin-21