IgG4-related disease: a complex under-diagnosed clinical entity

Rheumatol Int. 2018 Feb;38(2):169-177. doi: 10.1007/s00296-017-3765-7. Epub 2017 Jul 5.

Abstract

IgG4-related disease (IgG4-RD) encompasses a spectrum of complex fibro-inflammatory disorders which are often under diagnosed due to unfamiliarity by clinicians. A challenging multitude of clinical manifestations makes the diagnosis cumbersome. The primary clinical feature in IgG4-RD entails a tumor-like presentation coupled with tissue-destructive lesions. Histopathological findings include lymphoplasmacytic infiltrate, storiform fibrosis, and obliterative phlebitis. These findings, in combination with elevated serum immunoglobulin G4 levels, are diagnostic in the setting of single- or multi-organ involvement. A closer understanding of the role of T cells and B cells in the increased production of IgG4 has led to a notion that IgG4 can act as a pathogen, anti-inflammatory agent, or rheumatoid factor. Glucocorticoids are the primary treatment modality; however, relapse is common with prolonged therapy. Alternatively, immunomodulatory agents are being increasingly used as therapy. The aim of this article is to raise awareness of IgG4-RD and review the diagnostic algorithm, as IgG4-RD often mimics a wide array of clinical conditions. In addition, we summarize the pathogenesis and current treatment guidelines of IgG4-RD for clinicians. Awareness and accurate diagnosis are crucial in preventing progression to chronic diseases, thereby diminishing disease-related morbidity and mortality.

Keywords: AIP; Fibro-inflammatory disease; IgG4; IgG4-RD; Review.

Publication types

  • Review

MeSH terms

  • Algorithms
  • Animals
  • Autoimmune Diseases / diagnosis
  • Autoimmune Diseases / drug therapy
  • Autoimmune Diseases / immunology*
  • Autoimmunity* / drug effects
  • Biomarkers / blood
  • Clinical Decision-Making
  • Diagnosis, Differential
  • Fibrosis
  • Glucocorticoids / therapeutic use
  • Humans
  • Immunoglobulin G / blood
  • Immunoglobulin G / immunology*
  • Immunosuppressive Agents / therapeutic use
  • Inflammation / diagnosis
  • Inflammation / drug therapy
  • Inflammation / immunology*
  • Predictive Value of Tests
  • Risk Factors
  • Treatment Outcome

Substances

  • Biomarkers
  • Glucocorticoids
  • Immunoglobulin G
  • Immunosuppressive Agents