Transient hemolysis due to anti-D and anti-A1 produced by engrafted donor's lymphocytes after allogeneic unmanipulated haploidentical hematopoietic stem cell transplantation

Transfusion. 2017 Oct;57(10):2355-2358. doi: 10.1111/trf.14232. Epub 2017 Jul 13.

Abstract

Background: Development of de novo alloantibodies against recipient's red blood cell (RBC) antigens by engrafted donor's lymphocytes is a known phenomenon in the setting of allogeneic hematopoietic stem cell transplantation (HSCT). This situation is usually clinically insignificant. We report a case of early clinically relevant hemolytic anemia in a blood group A1 D+ patient, due to a limited production of anti-D and anti-A1 produced by nonpreviously sensitized newly engrafted donor's immune system.

Case report: A 31-year-old Caucasian woman, blood group A1 , D+, with Hodgkin's lymphoma, received an unmanipulated haploidentical allogeneic peripheral blood HSCT after a nonmyeloablative conditioning regimen. Donor blood group was A2 B, D-. The patient had an uneventful course until Day +34, when she developed clinically significant hemolytic anemia with a positive direct antiglobulin test. Anti-D and anti-A1 produced by the donor-engrafted lymphocytes were detected both in serum and in eluate. The hemolysis produced an accelerated group change, turning the patient's ABO group into A2 B 2 weeks after the detection of the alloantibodies. As the residual patient's RBCs progressively disappeared, anti-D and anti-A1 production decreased and were not detected in serum by Day +41.

Conclusion: This case illustrates that de novo alloantibody production against ABO and D antigens by the newly engrafted donor's lymphocytes can occasionally cause clinically significant anemia. To our knowledge, this is the first case reported of clinically significant hemolytic anemia due to a transient anti-D anti-A1 alloimmunization after T-cell-repleted haploidentical HSCT.

Publication types

  • Case Reports

MeSH terms

  • ABO Blood-Group System / immunology
  • Adult
  • Anemia, Hemolytic / etiology*
  • Blood Group Incompatibility
  • Female
  • Graft Survival
  • Hematopoietic Stem Cell Transplantation / adverse effects*
  • Humans
  • Isoantibodies / biosynthesis*
  • Isoantibodies / blood
  • Lymphocytes / immunology*
  • Rho(D) Immune Globulin / biosynthesis*

Substances

  • ABO Blood-Group System
  • Isoantibodies
  • RHO(D) antibody
  • Rho(D) Immune Globulin