Id genes are essential for early heart formation

Genes Dev. 2017 Jul 1;31(13):1325-1338. doi: 10.1101/gad.300400.117. Epub 2017 Aug 9.

Abstract

Deciphering the fundamental mechanisms controlling cardiac specification is critical for our understanding of how heart formation is initiated during embryonic development and for applying stem cell biology to regenerative medicine and disease modeling. Using systematic and unbiased functional screening approaches, we discovered that the Id family of helix-loop-helix proteins is both necessary and sufficient to direct cardiac mesoderm formation in frog embryos and human embryonic stem cells. Mechanistically, Id proteins specify cardiac cell fate by repressing two inhibitors of cardiogenic mesoderm formation-Tcf3 and Foxa2-and activating inducers Evx1, Grrp1, and Mesp1. Most importantly, CRISPR/Cas9-mediated ablation of the entire Id (Id1-4) family in mouse embryos leads to failure of anterior cardiac progenitor specification and the development of heartless embryos. Thus, Id proteins play a central and evolutionarily conserved role during heart formation and provide a novel means to efficiently produce cardiovascular progenitors for regenerative medicine and drug discovery applications.

Keywords: CRISPR/Cas9-mediated quadruple knockout; Id proteins; cardiac mesoderm specification; cardiac progenitors; heartless; platform for cardiac disease modeling and drug discovery.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Basic Helix-Loop-Helix Transcription Factors / genetics
  • Cell Differentiation / genetics
  • Cell Line
  • Cell Lineage / genetics*
  • Embryo, Mammalian / cytology
  • Embryo, Mammalian / embryology
  • Embryo, Nonmammalian / cytology
  • Embryo, Nonmammalian / embryology
  • Embryonic Stem Cells / cytology
  • Embryonic Stem Cells / physiology
  • Gene Editing
  • Gene Expression Regulation, Developmental / genetics
  • Heart / embryology*
  • Heart Defects, Congenital / genetics
  • Humans
  • Inhibitor of Differentiation Proteins / genetics*
  • Inhibitor of Differentiation Proteins / metabolism*
  • Mesoderm / cytology
  • Mesoderm / physiology
  • Mice
  • Mutation
  • Organogenesis / genetics*
  • Seeds
  • Xenopus laevis / embryology

Substances

  • Basic Helix-Loop-Helix Transcription Factors
  • Inhibitor of Differentiation Proteins