Anti-neutrophil Cytoplasmic Antibody-associated Vasculitis (AAV) Restricted to the Limbs

Intern Med. 2018 May 1;57(9):1301-1308. doi: 10.2169/internalmedicine.9848-17. Epub 2017 Dec 27.

Abstract

A previously healthy 58-year-old man was admitted for muscle pain and weakness [manual muscle testing (MMT) of 4/4 for upper and lower limbs]. We detected elevated levels of inflammatory makers and PR3-anti-neutrophil cytoplasmic antibody (ANCA). Subsequently, the muscle weakness rapidly progressed to an MMT of 2 for all limbs. Magnetic resonance imaging indicated muscle edema, and the creatine kinase (CK) level increased to 29,998 U/L. Methylprednisolone (mPSL) and cyclophosphamide pulse therapy improved the patient symptoms. MMT recovered to 4 for all limbs. A muscle biopsy showed degenerated muscle fibers surrounded by neutrophil-predominant infiltration. In addition, lamina elastic breakdown and fibrinoid necrosis of arterioles were observed. A final diagnosis of microscopic polyangiitis (MPA) limited to the muscles was made.

Keywords: ANCA-associated vasculitis,; PR3-ANCA; organ limited vasculitis.

Publication types

  • Case Reports

MeSH terms

  • Anti-Neutrophil Cytoplasmic Antibody-Associated Vasculitis / immunology
  • Anti-Neutrophil Cytoplasmic Antibody-Associated Vasculitis / physiopathology*
  • Antibodies, Antineutrophil Cytoplasmic / blood*
  • Antibodies, Antineutrophil Cytoplasmic / immunology*
  • Asian People
  • Biomarkers / blood
  • Cyclophosphamide / therapeutic use*
  • Humans
  • Inflammation / blood
  • Lower Extremity / physiopathology
  • Male
  • Microscopic Polyangiitis / diagnosis*
  • Middle Aged
  • Muscle Weakness / drug therapy*
  • Muscle Weakness / physiopathology
  • Myeloblastin / blood
  • Myeloblastin / immunology
  • Peroxidase / immunology
  • Prednisolone / therapeutic use*
  • Treatment Outcome
  • Upper Extremity / physiopathology

Substances

  • Antibodies, Antineutrophil Cytoplasmic
  • Biomarkers
  • Cyclophosphamide
  • Prednisolone
  • Peroxidase
  • Myeloblastin