Inhibition of RGMa alleviates symptoms in a rat model of neuromyelitis optica

Sci Rep. 2018 Jan 8;8(1):34. doi: 10.1038/s41598-017-18362-2.

Abstract

Neuromyelitis optica (NMO) is an autoimmune disease associated with NMO immunoglobulin G (NMO-IgG), an antibody that selectively binds to the aquaporin-4. Here, we established a localized NMO model by injecting NMO-IgG into the spinal cord, and assessed the efficacy of treating its NMO-like symptoms by blocking repulsive guidance molecule-a (RGMa), an axon growth inhibitor. The model showed pathological features consistent with NMO. Systemic administration of humanized monoclonal anti-RGMa antibody delayed the onset and attenuated the severity of clinical symptoms. Further, it preserved astrocytes and reduced inflammatory-cell infiltration and axonal damage, suggesting that targeting RGMa is effective in treating NMO.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Aquaporin 4 / genetics
  • Aquaporin 4 / metabolism
  • Astrocytes / metabolism
  • Autoimmunity
  • CD4-Positive T-Lymphocytes / immunology
  • CD4-Positive T-Lymphocytes / metabolism
  • Disease Models, Animal
  • GPI-Linked Proteins
  • Gene Expression
  • Glial Fibrillary Acidic Protein / genetics
  • Glial Fibrillary Acidic Protein / metabolism
  • Humans
  • Immunoglobulin G / immunology*
  • Immunoglobulin G / pharmacology
  • Membrane Proteins / antagonists & inhibitors
  • Membrane Proteins / immunology*
  • Nerve Tissue Proteins / antagonists & inhibitors
  • Nerve Tissue Proteins / immunology*
  • Neuromyelitis Optica / diagnosis
  • Neuromyelitis Optica / drug therapy
  • Neuromyelitis Optica / immunology*
  • Neuromyelitis Optica / metabolism
  • Neurons / immunology
  • Neurons / metabolism
  • Rats
  • Severity of Illness Index
  • Spinal Cord / immunology
  • Spinal Cord / metabolism
  • Spinal Cord / pathology
  • Th17 Cells / immunology
  • Th17 Cells / metabolism

Substances

  • Aquaporin 4
  • GFAP protein, rat
  • GPI-Linked Proteins
  • Glial Fibrillary Acidic Protein
  • Immunoglobulin G
  • Membrane Proteins
  • Nerve Tissue Proteins
  • RGMA protein, rat