Haematopoietic stem cell transplantation for mucopolysaccharidosis type VII: A case report

Pediatr Transplant. 2018 Nov;22(7):e13278. doi: 10.1111/petr.13278. Epub 2018 Aug 9.

Abstract

Mucopolysaccharidosis type VII (MPS VII) is an inherited disease characterized by the cellular accumulation of undegraded GAGs due to the deficiency of the lysosomal enzyme β-glucuronidase. We describe a case of a 2-year-old female affected by a moderate form of MPS VII and submitted twice to HSCT with the aim of stabilizing skeletal problems and preventing neurocognitive alterations. The child underwent a second transplantation due to the rejection of the graft after a reduced-intensity conditioning in the first transplant. A myeloablative regimen allowed to achieve a stable full donor engraftment and normal enzyme levels during the 6 years of follow-up. Clinically, we observed stabilization of skeletal deformities and normal neurocognitive development. This is one of the few reports of mucopolysaccharidosis type VII treated with allogeneic HSCT.

Keywords: developmental; genetics; haematopoietic stem cell transplantation; metabolic disorders; neurology.

Publication types

  • Case Reports

MeSH terms

  • Child, Preschool
  • Female
  • Hematopoietic Stem Cell Transplantation*
  • Humans
  • Mucopolysaccharidosis VII / therapy*