Lung injury and fibrosis induced by a mutant form of surfactant protein C

J Clin Invest. 2018 Aug 31;128(9):3745-3746. doi: 10.1172/JCI122727. Epub 2018 Aug 13.

Abstract

Although mutant forms of the gene encoding surfactant protein C (SFTPC) have been linked to interstitial lung disease, the mechanisms by which the most common of these mutations, SFTPCI73T, results in lung fibrosis are uncertain. In this issue of the JCI, Nureki et al. developed a knockin mouse model and showed that SFTPCI73T is expressed by alveolar type II (AT2) epithelial cells in the lungs. These mice developed an age-related fibrotic phenotype when the mutant allele was expressed at low levels and acute lung inflammation/injury followed by lung fibrosis when mutant SFTPCI73T expression was enhanced. This work provides important information regarding the impact of AT2 cell dysfunction on fibrotic remodeling in the lungs.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, U.S. Gov't, Non-P.H.S.
  • Comment

MeSH terms

  • Animals
  • Fibrosis
  • Lung
  • Lung Injury*
  • Mice
  • Protein C
  • Pulmonary Fibrosis*
  • Surface-Active Agents

Substances

  • Protein C
  • Surface-Active Agents