The Power of Proficiency Testing: Unraveling Single-Nucleotide Polymorphism Interference, With Potential Impact on Clinical Testing of Spinocerebellar Ataxia Type 3

Arch Pathol Lab Med. 2019 Mar;143(3):349-355. doi: 10.5858/arpa.2017-0566-OA. Epub 2018 Nov 1.

Abstract

Context.—: The College of American Pathologists proficiency testing program has been instrumental in identifying problems in clinical testing.

Objective.—: To describe how this program was used to identify a single-nucleotide polymorphism that affects clinical testing for spinocerebellar ataxia type 3.

Design.—: A proficiency testing sample with discordant results for spinocerebellar ataxia type 3 analysis was further evaluated by targeted Sanger sequencing and genotype polymerase chain reaction using multiple DNA polymerases.

Results.—: Of 28 laboratories responding in the spinocerebellar ataxia type 3 Proficiency Survey, 18 reported an incorrect homozygous result and 10 reported the expected heterozygous result. A heterozygous single-nucleotide polymorphism complementary to the 3' end of a published forward primer was identified in the proficiency testing sample, which may have led to allele dropout. However, this primer was used by only 3 of 18 laboratories (16%) reporting a homozygous result. A new forward primer of identical sequence, except for the 3' end being complementary to the single-nucleotide polymorphism, showed the expected heterozygous pattern. The possibility of DNA polymerase 3'-5' exonuclease activity contributing to allele dropout was investigated by testing 9 additional polymerases with and without exonuclease activity. No clear pattern emerged, but enzymes with and without 3'-5' exonuclease activity yielded both homozygous and expected heterozygous results with the published forward primer.

Conclusions.—: Proactive systematic primer sequence checking is recommended because single-nucleotide polymorphism interference may result in allele dropout and impact clinical testing. Allele dropout is also influenced by other factors, including DNA polymerase exonuclease activity.

MeSH terms

  • Genetic Testing / methods
  • Genetic Testing / standards*
  • Humans
  • Laboratory Proficiency Testing*
  • Machado-Joseph Disease / diagnosis*
  • Machado-Joseph Disease / genetics*
  • Polymerase Chain Reaction / methods
  • Polymerase Chain Reaction / standards
  • Polymorphism, Single Nucleotide