Glaucoma in Phacomatosis Pigmentovascularis in a Young African Adolescent Boy: A Case Report

J Glaucoma. 2019 Jul;28(7):e124-e125. doi: 10.1097/IJG.0000000000001264.

Abstract

Background: Phacomatosis pigmentovascularis (PPV) has previously almost exclusively been reported in Asians and in dermatological journals. In this report, we present a case of a young black South African adolescent boy referred to our eye clinic.

Case report: A 15-year-old male patient presented with gradual, painless loss of vision in his right eye. Clinical examination revealed a port-wine stain with ocular involvement on the right as well as a nevus of Ota. Fundoscopy on the right revealed an advanced glaucomatous optic disc and raised intraocular pressure. A diagnosis of glaucoma associated with PPV was made.

Conclusion: We present the first case of PPV in an African male individual with associated glaucoma seen at our tertiary hospital.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Antihypertensive Agents / therapeutic use
  • Black People / ethnology
  • Glaucoma, Open-Angle / diagnosis
  • Glaucoma, Open-Angle / drug therapy
  • Glaucoma, Open-Angle / etiology*
  • Gonioscopy
  • Humans
  • Intraocular Pressure / physiology
  • Male
  • Nerve Fibers / pathology
  • Neurocutaneous Syndromes / complications*
  • Neurocutaneous Syndromes / ethnology
  • Nevus of Ota / diagnosis
  • Optic Disk / pathology
  • Port-Wine Stain / diagnosis
  • Retinal Ganglion Cells / pathology
  • South Africa / epidemiology
  • Timolol / therapeutic use
  • Tomography, Optical Coherence
  • Ultrasonography

Substances

  • Antihypertensive Agents
  • Timolol

Supplementary concepts

  • Phacomatosis pigmentovascularis