DNAJC proteins and pathways to parkinsonism

FEBS J. 2019 Aug;286(16):3080-3094. doi: 10.1111/febs.14936. Epub 2019 Jun 20.

Abstract

The DNAJC protein family is a subclass of heat shock proteins that has attracted recent attention due to the identification of mutations that are linked with parkinsonism, a feature of Parkinson's disease and other neurological disorders. In this review, we discuss the current genetic and functional evidence of the association of these DNAJC proteins with disease and how mutations in these proteins may contribute to disease pathogenesis. Although DNAJC6 (Auxilin), DNAJC12, and DNAJC5 (CSPα) exhibit strong genetic association with disease, DNAJC26 (GAK), DNAJC13 (RME-8), and DNAJC10 (Erdj5) require additional evidence to definitively link reported variants to parkinsonism. Remarkably, multiple DNAJC proteins (Auxilin, GAK, RME-8, CSPα) functionally converge on pathways of synaptic trafficking and clathrin dynamics, highlighting an important role of those pathways in the pathogenesis of parkinsonism. Further research is required to define the mechanisms through which these mutations contribute to disease etiology.

Keywords: DNAJ; GAK; Auxilin; CSPα; DNAJC10; Erdj5; Hsc70; RME-8; clathrin; parkinsonisms.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Genetic Association Studies
  • Genetic Predisposition to Disease*
  • HSC70 Heat-Shock Proteins / genetics*
  • HSP40 Heat-Shock Proteins / genetics
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics
  • Membrane Proteins / genetics
  • Molecular Chaperones / genetics
  • Mutation / genetics
  • Parkinsonian Disorders / genetics*
  • Parkinsonian Disorders / pathology
  • Protein Serine-Threonine Kinases / genetics
  • Repressor Proteins / genetics

Substances

  • DNAJC10 protein, human
  • DNAJC12 protein, human
  • DNAJC13 protein, human
  • DNAJC6 protein, human
  • HSC70 Heat-Shock Proteins
  • HSP40 Heat-Shock Proteins
  • Intracellular Signaling Peptides and Proteins
  • Membrane Proteins
  • Molecular Chaperones
  • Repressor Proteins
  • cysteine string protein
  • GAK protein, human
  • Protein Serine-Threonine Kinases