Mutational landscape of patients with acute promyelocytic leukemia at diagnosis and relapse

Am J Hematol. 2019 Oct;94(10):1091-1097. doi: 10.1002/ajh.25573. Epub 2019 Jul 23.

Abstract

Despite the high probability of cure of patients with acute promyelocytic leukemia (APL), mechanisms of relapse are still largely unclear. Mutational profiling at diagnosis and/or relapse may help to identify APL patients needing frequent molecular monitoring and early treatment intervention. Using an NGS approach including a 31 myeloid gene-panel, we tested BM samples of 44 APLs at the time of diagnosis, and of 31 at relapse. Mutations in PML and RARA genes were studied using a customized-NGS-RNA panel. Patients relapsing after ATRA-chemotherapy rarely had additional mutations (P = .009). In patients relapsing after ATRA/ATO, the PML gene was a preferential mutation target. We then evaluated the predictive value of mutations at APL diagnosis. A median of two mutations was detectable in 9/11 patients who later relapsed, vs one mutation in 21/33 patients who remained in CCR (P = .0032). This corresponded to a significantly lower risk of relapse in patients with one or less mutations (HR 0.046; 95% CI 0.011-0.197; P < .0001). NGS-analysis at the time of APL diagnosis may inform treatment decisions, including alternative treatments for cases with an unfavorable mutation profile.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Arsenic Trioxide / administration & dosage
  • Arsenic Trioxide / pharmacology
  • Bone Marrow / pathology
  • Clone Cells
  • Disease Progression
  • Drug Resistance, Neoplasm
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Leukemia, Promyelocytic, Acute / drug therapy
  • Leukemia, Promyelocytic, Acute / genetics*
  • Mutation*
  • Neoplasm Proteins / genetics
  • Neoplastic Stem Cells
  • Oncogene Proteins, Fusion / genetics*
  • Promyelocytic Leukemia Protein / genetics*
  • Protein Domains / genetics
  • RNA, Messenger / genetics*
  • RNA, Neoplasm / genetics*
  • Recurrence
  • Remission Induction
  • Reproducibility of Results
  • Retinoic Acid Receptor alpha / genetics*
  • Tretinoin / administration & dosage

Substances

  • Neoplasm Proteins
  • Oncogene Proteins, Fusion
  • Promyelocytic Leukemia Protein
  • RARA protein, human
  • RNA, Messenger
  • RNA, Neoplasm
  • Retinoic Acid Receptor alpha
  • promyelocytic leukemia-retinoic acid receptor alpha fusion oncoprotein
  • PML protein, human
  • Tretinoin
  • Arsenic Trioxide