Primary iliocaval leiomyosarcomas: The path beyond surgery

Eur J Surg Oncol. 2020 May;46(5):893-897. doi: 10.1016/j.ejso.2020.01.034. Epub 2020 Feb 6.

Abstract

Introduction: Iliocaval leiomyosarcoma (ICLM) is a rare and aggressive form of sarcoma within the retroperitoneum. Surgery is the mainstay of treatment, with no consensus on the benefit of chemoradiotherapy in the neo/adjuvant setting. This study aims to describe the natural history of a chemotherapy-naïve ICLM treated in a tertiary cancer centre and to explore potential directions to improve oncological outcome.

Materials and methods: A prospective database was used to identify patient demographics, clinicopathological variables and oncological outcomes in 30 patients who underwent surgical resection in our institution for primary non-metastatic ICLM between 2003 and 2018.

Results: There was no 90-day mortality. With a median follow-up time of 70.0 months (95% CI 52.6-87.4), 5/30 patients (16.7%) developed local recurrence while 11/30 (36.7%) developed distant metastatic disease. 1 patient (3.3%) developed both local and distant recurrence. Median overall survival of our cohort was 41.0 months (95% CI 33.6-48.4) and 5-year overall survival rate was 32.1%. Multivariate survival analysis using the Cox proportional hazard model identified tumour grade and blood loss of more than 600 mL as key prognostic factors in our model.

Conclusion: Management of ICLM should be centralised in high-volume sarcoma centres with expertise in the management of retroperitoneal sarcomas. Integration of tumour biology with a concerted effort to conduct conclusive multi-centre phase III in histological and molecularly defined sarcoma subgroups is necessary to improve patient outcome. We eagerly await the results of STRASS 2 study to gain more insights to the efficacy of neoadjuvant chemotherapy on patient prognosis.

Keywords: Chemotherapy; Iliocaval leiomyosarcoma; Inferior vena cava; Radiotherapy; Retroperitoneum; Surgery.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Blood Loss, Surgical
  • Female
  • Humans
  • Iliac Vein / pathology
  • Iliac Vein / surgery*
  • Leiomyosarcoma / pathology
  • Leiomyosarcoma / surgery*
  • Male
  • Margins of Excision
  • Middle Aged
  • Multivariate Analysis
  • Neoplasm Grading
  • Neoplasm Recurrence, Local
  • Operative Time
  • Plastic Surgery Procedures
  • Proportional Hazards Models
  • Retroperitoneal Neoplasms / pathology
  • Retroperitoneal Neoplasms / surgery*
  • Survival Rate
  • Vascular Neoplasms / pathology
  • Vascular Neoplasms / surgery*
  • Vascular Surgical Procedures
  • Vena Cava, Inferior / pathology
  • Vena Cava, Inferior / surgery*