Primary DQ effect in the association between HLA and neurological syndromes with anti-GAD65 antibodies

J Neurol. 2020 Jul;267(7):1906-1911. doi: 10.1007/s00415-020-09782-8. Epub 2020 Mar 9.

Abstract

The primary cause of neurological syndromes with antibodies against glutamic acid decarboxylase 65 (GAD65-Ab) is unknown, but genetic predisposition may exist as it is suggested by the co-occurrence in patients and their relatives of other organ-specific autoimmune diseases, notably type 1 diabetes mellitus (T1DM), and by the reports of a few familial cases. We analyzed the human leukocyte antigen (HLA) in 32 unrelated patients and compared them to an ethnically matched sample of 137 healthy controls. Four-digit resolution HLA alleles were imputed from available Genome Wide Association data, and full HLA next-generation sequencing-based typing was also performed. HLA DQA1*05:01-DQB1*02:01-DRB1*03:01 was the most frequent class II haplotype in patients (13/32, 41%). DQB1*02:01 was the only allele found to be significantly more common in patients than in controls (20/137, 15%, corrected p = 0.03, OR 3.96, 95% CI [1.54-10.09]). There was also a trend towards more frequent DQA1*05:01 among patients compared to controls (22/137, 16%; corrected p = 0.05, OR 3.54, 95% CI [1.40-8.91]) and towards a protective effect of DQB1*03:01 (2/32, 6% in patients vs. 42/137, 31% in control group; corrected p = 0.05, OR 0.15, 95% CI [0.02-0.65]). There was no significant demographic or clinical difference between DQ2 and non-DQ2 carriers (p > 0.05). Taken together, these findings suggest a primary DQ effect on GAD65-Ab neurological diseases, partially shared with other systemic organ-specific autoimmune diseases such as T1DM. However, it is likely that other non-HLA loci are involved in the genetic predisposition of GAD65-Ab neurological syndromes.

Keywords: Cerebellar ataxia; Glutamic acid decarboxylase; HLA; Limbic encephalitis; Stiff person syndrome.

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Autoantibodies* / blood
  • Autoantibodies* / cerebrospinal fluid
  • Cerebellar Ataxia* / genetics
  • Cerebellar Ataxia* / immunology
  • Cerebellar Ataxia* / metabolism
  • Comorbidity
  • Diabetes Mellitus, Type 1* / genetics
  • Diabetes Mellitus, Type 1* / immunology
  • Diabetes Mellitus, Type 1* / metabolism
  • Female
  • Genetic Predisposition to Disease
  • Glutamate Decarboxylase / immunology*
  • HLA-DQ Antigens / genetics*
  • HLA-DQ alpha-Chains / genetics
  • HLA-DQ beta-Chains / genetics
  • HLA-DRB1 Chains / genetics
  • Haplotypes
  • Humans
  • Limbic Encephalitis* / genetics
  • Limbic Encephalitis* / immunology
  • Limbic Encephalitis* / metabolism
  • Male
  • Middle Aged
  • Stiff-Person Syndrome* / genetics
  • Stiff-Person Syndrome* / immunology
  • Stiff-Person Syndrome* / metabolism
  • Young Adult

Substances

  • Autoantibodies
  • HLA-DQ Antigens
  • HLA-DQ alpha-Chains
  • HLA-DQ beta-Chains
  • HLA-DQA1 antigen
  • HLA-DQB1 antigen
  • HLA-DRB1 Chains
  • Glutamate Decarboxylase
  • glutamate decarboxylase 2